Sarantaus L, Auranen A, Nevanlinna H
Department of Obstetrics and Gynecology, Helsinki University Central Hospital, Haartmaninkatu 2, FIN-00029 HUCH, Finland.
Int J Oncol. 2001 Apr;18(4):831-5. doi: 10.3892/ijo.18.4.831.
Germ-line mutations in BRCA1 and BRCA2 predispose to hereditary breast-ovarian cancer syndrome. In Finland, 21 different BRCA1/2 mutations have been identified and 14 of the mutations are founders that account for the great majority of all BRCA1/2 mutations. Our aim was to determine the prevalence of the 21 BRCA1/2 mutations in Finnish ovarian carcinoma families. Mutations were screened in 23 families with at least two cases of invasive epithelial ovarian carcinoma in the first-degree relatives. The families had been identified from a population-based series of 559 Finnish epithelial ovarian carcinoma patients. Fourteen of the families were site-specific ovarian carcinoma families, while breast cancer was present in nine families. Mutations were detected in five families: two had a mutation in BRCA1 and three in BRCA2. In one family, a novel, apparently disease-causing missense mutation in the BRCA2 gene had been identified previously. Thus, 26% of the Finnish ovarian carcinoma families were found to be BRCA1/2 mutation-positive. Strong ovarian cancer family history and early-onset breast cancer were strongly associated with BRCA1/2 mutation status; all families with three ovarian carcinoma cases or early-onset breast cancer (<50 years) were mutation-positive, whereas all families with later-onset breast cancer as well as the majority (9/11) of the site-specific ovarian carcinoma families with minor ovarian cancer history (i.e. two affected cases) remained mutation-negative.
BRCA1和BRCA2基因的种系突变易导致遗传性乳腺癌-卵巢癌综合征。在芬兰,已鉴定出21种不同的BRCA1/2突变,其中14种突变是始祖突变,占所有BRCA1/2突变的绝大多数。我们的目的是确定芬兰卵巢癌家族中这21种BRCA1/2突变的患病率。对23个家族进行了突变筛查,这些家族的一级亲属中至少有两例浸润性上皮性卵巢癌病例。这些家族是从559例芬兰上皮性卵巢癌患者的基于人群的系列中确定的。其中14个家族是特定部位卵巢癌家族,9个家族存在乳腺癌。在5个家族中检测到突变:2个家族BRCA1有突变,3个家族BRCA2有突变。在一个家族中,先前已鉴定出BRCA2基因中一种新的、明显致病的错义突变。因此,发现26%的芬兰卵巢癌家族BRCA1/2突变呈阳性。强烈的卵巢癌家族史和早发性乳腺癌与BRCA1/2突变状态密切相关;所有有三例卵巢癌病例或早发性乳腺癌(<50岁)的家族均为突变阳性,而所有晚发性乳腺癌家族以及大多数(9/11)有轻微卵巢癌病史(即两例受影响病例)的特定部位卵巢癌家族仍为突变阴性。