Chen Chun-Hsiung, Chen Chih-Hsueh, Chen Horng-An, Liao Hsien-Tzung, Lin Hsiao-Yi
Veterans General Hospital, Taipei and National Yang-Ming Medical University, Taiwan.
J Clin Rheumatol. 2006 Oct;12(5):252-4. doi: 10.1097/01.rhu.0000239902.91768.f9.
Multicentric reticulohistiocytosis (MRH) is a rare multisystemic disease presenting with skin lesions and erosive polyarthritis and is often associated with malignancy. We describe a 60-year-old woman with diffuse papulonodular skin eruptions and progressive osteolytic bone damage over the bilateral hands, humeral head, and acromioclavicular joints within 2 years. Moreover, dysphagia and a hoarse voice occurred in this patient and an unusual huge mass-reticulohistiocytoma--developed over the left upper back. Tissue biopsy of the skin lesions, laryngeal nodules, and this large mass showed infiltration of numerous CD68(+) histiocytes and multinucleated giant cells with abundant eosinophilic ground-glass cytoplasm. Combination therapy with steroids and methotrexate improved her cutaneous, joint, and laryngopharyngeal symptoms. The large reticulohistiocytoma resolved with methylprednisolone pulse therapy. This polyarthritis, which can be confused with rheumatoid arthritis, can be diagnosed by careful immunohistochemical examination of biopsies. To prevent the irreversible disease process, early and aggressive therapy is necessary.
多中心网状组织细胞增生症(MRH)是一种罕见的多系统疾病,表现为皮肤病变和侵蚀性多关节炎,常与恶性肿瘤相关。我们描述了一名60岁女性,在2年内双手、肱骨头和肩锁关节出现弥漫性丘疹结节性皮肤疹和进行性溶骨性骨损害。此外,该患者出现吞咽困难和声音嘶哑,左上背部出现一个不寻常的巨大肿物——网状组织细胞瘤。皮肤病变、喉部结节和这个大肿物的组织活检显示大量CD68(+)组织细胞和多核巨细胞浸润,胞质丰富,呈嗜酸性毛玻璃样。类固醇和甲氨蝶呤联合治疗改善了她的皮肤、关节和咽喉症状。大的网状组织细胞瘤经甲基强的松龙冲击治疗后消退。这种可能与类风湿关节炎混淆的多关节炎,可通过对活检组织进行仔细的免疫组化检查来诊断。为防止疾病进程不可逆,早期积极治疗是必要的。