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两只惠比特犬中与遗传性磷酸果糖激酶缺乏相关的溶血、肌病和心脏病

Hemolysis, myopathy, and cardiac disease associated with hereditary phosphofructokinase deficiency in two Whippets.

作者信息

Gerber Karen, Harvey John W, D'Agorne Sara, Wood Jonathan, Giger Urs

机构信息

Axiom Veterinary Laboratory, Newton Abbott, UK.

出版信息

Vet Clin Pathol. 2009 Mar;38(1):46-51. doi: 10.1111/j.1939-165X.2008.00089.x. Epub 2008 Oct 28.

Abstract

Two male castrated Whippet littermates were presented at 1 year of age for pallor, tachycardia, systolic heart murmur, dark yellow to orange feces, intermittent lethargy, pigmenturia, and muscle shivering or cramping after exercise. Persistent macrocytic hypochromic anemia with marked reticulocytosis and metarubricytosis was found when CBC results were compared with reference values for Whippets. Increased serum creatine kinase activity and hyperkalemia also were sometimes present over the 4-year period of evaluation. Progressively increasing serum concentrations of N-terminal prohormone brain natriuretic peptide suggested cardiac disease. Erythrocytes from the whippets were less osmotically fragile but more alkaline fragile than those from control dogs. Erythrocyte phosphofructokinase (PFK) activities and 2,3-diphosphoglycerate concentrations were decreased. Restriction enzyme-based DNA test screening and DNA sequencing revealed the same mutation in the muscle-PFK gene of the Whippets as seen in English Springer Spaniel dogs with PFK deficiency. This is the first report of PFK deficiency in Whippet dogs. In addition to causing hemolysis and exertional myopathy, heart disease may be a prominent clinical component of PFK deficiency in this breed and has not been previously recognized in PFK-deficient English Springer Spaniels.

摘要

两只1岁的雄性去势惠比特犬同窝幼犬因面色苍白、心动过速、收缩期心脏杂音、深黄色至橙色粪便、间歇性嗜睡、色素尿以及运动后肌肉颤抖或痉挛前来就诊。将全血细胞计数(CBC)结果与惠比特犬的参考值进行比较时,发现存在持续性大细胞低色素性贫血,并伴有明显的网织红细胞增多和晚幼红细胞增多。在4年的评估期内,有时还会出现血清肌酸激酶活性升高和高钾血症。血清N末端脑钠肽前体浓度逐渐升高提示存在心脏疾病。与对照犬相比,惠比特犬的红细胞对渗透压的耐受性更强,但对碱性环境更敏感。红细胞磷酸果糖激酶(PFK)活性和2,3-二磷酸甘油酸浓度降低。基于限制性内切酶的DNA检测筛选和DNA测序显示,惠比特犬肌肉PFK基因中的突变与患有PFK缺乏症的英国激飞猎犬相同。这是关于惠比特犬PFK缺乏症的首次报道。除了导致溶血和运动性肌病外,心脏病可能是该品种PFK缺乏症的一个突出临床特征,而在PFK缺乏的英国激飞猎犬中此前尚未被认识到。

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