Stannard V A, Fowler C, Robinson L, Besner G, Glick P L, Allen J E, Jewett T C, Cooney D R
Department of Surgery, University at Buffalo, State University of New York.
J Pediatr Surg. 1991 May;26(5):591-4. doi: 10.1016/0022-3468(91)90714-5.
Multifactorial sex-modified inheritance has been proposed as the model of transmission in familial Hirschsprung's disease (HD). A review of two separate kindreds suggests that aganglionosis may be inherited as an X-linked recessive or an autosomal dominant trait. Chromosomal anomalies and other syndromes, including G6PD deficiency, may occur with familial HD. Recurrence risk counseling for family members depends on accurate pedigree analysis and a comprehensive understanding of the genetic factors involved.
多因素性连锁修饰遗传已被提出作为家族性先天性巨结肠症(HD)的遗传模式。对两个独立家系的回顾表明,无神经节症可能作为X连锁隐性或常染色体显性性状遗传。家族性HD可能伴有染色体异常和其他综合征,包括葡萄糖-6-磷酸脱氢酶(G6PD)缺乏症。对家庭成员的复发风险咨询取决于准确的系谱分析和对相关遗传因素的全面理解。