Monge Matthieu, Chauveau Dominique, Cordonnier Carole, Noël Laure-Hélène, Presne Claire, Makdassi Raïfah, Jauréguy Maïté, Lecaque Caroline, Renou Marianne, Grünfeld Jean-Pierre, Choukroun Gabriel
From Departments of Nephrology-Dialysis-Transplantation (MM, CP, RM, MJ, CL, MR, GC) and Pathology (CC), CHU Amiens, Amiens; Department of Nephrology (DC), Rangueil Hospital, Toulouse; Departments of Pathology(LHN) and Nephrology (JPG), Necker Hospital, Paris; and ERI-12, INSERM (MM, GC), Jules Verne University, Amiens, France.
Medicine (Baltimore). 2011 May;90(3):212-222. doi: 10.1097/MD.0b013e31821cbdab.
Primary localized amyloidosis of the genitourinary tract is a rare entity characterized by small pseudotumors localized in the renal pelvis, ureters, or bladder. Amyloid fibrils are derived from immunoglobulin light chains, but no systemic plasma cell proliferation is detected. The clinical and radiologic features mimic urinary tract cancer, and local treatment is indicated. The prognosis is excellent in most cases, although disease recurrence is possible. We report 5 new cases of localized amyloidosis of the urinary tract, with lambda (4/5), or kappa (1/5) chain amyloid protein, involving the bladder (5/5), and the ureter and renal pelvis (1/5), with multiple, bilateral lesions in 1 case. The presenting complaint was painless hematuria in 4 cases. All cases were of primary (AL)-type amyloidosis. All patients underwent extensive investigation, and none presented any signs of generalized amyloidosis. A favorable outcome was observed in every case. We performed a comprehensive review of the literature, and summarize the data.
原发性泌尿生殖道局限性淀粉样变性是一种罕见的疾病,其特征为肾盂、输尿管或膀胱内出现局限性小假瘤。淀粉样纤维由免疫球蛋白轻链衍生而来,但未检测到系统性浆细胞增殖。其临床和放射学特征类似尿路癌,需进行局部治疗。多数病例预后良好,尽管疾病有可能复发。我们报告了5例新的尿路局限性淀粉样变性病例,其中4例为λ链淀粉样蛋白,1例为κ链淀粉样蛋白,病变累及膀胱(5例)、输尿管和肾盂(1例),1例为多发双侧病变。4例患者的主要症状为无痛性血尿。所有病例均为原发性(AL)型淀粉样变性。所有患者均接受了全面检查,均未出现全身性淀粉样变性的任何体征。所有病例均观察到良好的预后。我们对文献进行了全面回顾,并总结了相关数据。