Jamison Aaron, Crofts Kevin, Roberts Fiona, Gregory Maria Elena
a Tennent Institute of Ophthalmology, Gartnavel General Hospital , Glasgow , Scotland.
b Department of Ophthalmology , Stobhill Hospital , Glasgow , Scotland.
Orbit. 2016 Oct;35(5):254-7. doi: 10.1080/01676830.2016.1193529. Epub 2016 Aug 10.
This article reports a presentation of lacrimal sac rhinosporidiosis and informs the reader of this uncommon but important diagnosis. A 36-year-old man from Pakistan presented with a 3-month history of swelling at the nasal aspect of the left lower lid. This was associated with occasional crepitus and slight localised discomfort, but no epiphora. There was a palpable fullness near the left medial canthus associated with telecanthus but a normal sac washout and normal eye examination otherwise. Previous medical history included an ipsilateral nasal polypectomy and inferior meatal antrostomy around 10 years previously, whilst living in Pakistan. Various imaging modalities were useful in identifying a soft tissue mass within the left nasolacrimal duct. Following excision biopsy, histological examination confirmed the presence of rhinosporidiosis, likely caused by the organism Rhinosporidium seeberi. Rhinosporidiosis should be considered as a potential cause in any case of lacrimal sac pathology. Imaging studies may be helpful in measuring the extent of disease, although histological examination is required to confirm the diagnosis. Although rare, the complications of rhinosporidiosis can be potentially blinding or fatal. As discussed in this case, the presence of telecanthus may represent a lacrimal system tumour, either malignant or benign, and should always prompt further investigation.
本文报告了一例泪囊鼻孢子虫病的病例,并向读者介绍了这种罕见但重要的诊断。一名来自巴基斯坦的36岁男性,左下眼睑鼻侧肿胀3个月。伴有偶尔的捻发音和轻微的局部不适,但无溢泪。左内眦附近可触及饱满,伴有内眦间距增宽,但泪囊冲洗正常,眼部其他检查正常。既往病史包括大约10年前在巴基斯坦生活期间同侧鼻息肉切除术和下鼻道鼻窦造口术。各种影像学检查有助于发现左鼻泪管内的软组织肿块。切除活检后,组织学检查证实存在鼻孢子虫病,可能由西伯鼻孢子虫引起。在任何泪囊病变病例中,都应考虑鼻孢子虫病为潜在病因。影像学检查可能有助于评估疾病范围,不过确诊仍需组织学检查。尽管罕见,但鼻孢子虫病的并发症可能导致失明或死亡。如本病例所讨论的,内眦间距增宽可能提示泪器系统肿瘤,无论是恶性还是良性,均应进一步检查。