Dei-Adomakoh Yvonne A, Quarcoopome Leslie, Abrahams Afua D, Segbefia Catherine I, Dey Dzifa I
Department of Haematology, University of Ghana School of Biomedical and Allied Health Sciences, PO Box GP 4236, Accra, Ghana.
Korle Bu Teaching Hospital, Accra, Ghana.
Ghana Med J. 2018 Mar;52(1):61-65. doi: 10.4314/gmj.v52i1.9.
Castleman disease is a rare cause of lymphoid hyperplasia and may result in localized symptoms or an aggressive, multisystem disorder. It can mimic other diseases like lymphoma or tuberculosis. It classically presents as a mediastinal mass that involves the lymphatic tissue primarily but can also affect extra lymphatic sites including the lungs, larynx, parotid glands, pancreas, meninges, and muscles. In HIV and HHV8-negative patients with idiopathic multi-centric Castleman disease, pathogenesis may involve autoimmune mechanisms. We highlight and report a case of a 34-year-old Ghanaian female who was successfully diagnosed and managed for Sjögren's as well as plasma cell variant Castleman disease with combination chemotherapy and rituximab followed by eighteen months maintenance therapy with pulse chlorambucil and prednisolone and three monthly rituximab.
卡斯特曼病是淋巴组织增生的罕见病因,可导致局部症状或侵袭性多系统疾病。它可类似其他疾病,如淋巴瘤或结核病。其典型表现为纵隔肿块,主要累及淋巴组织,但也可影响肺、喉、腮腺、胰腺、脑膜和肌肉等淋巴外部位。在人类免疫缺陷病毒(HIV)和人疱疹病毒8(HHV8)阴性的特发性多中心卡斯特曼病患者中,发病机制可能涉及自身免疫机制。我们重点介绍并报告了一例34岁加纳女性患者,该患者成功诊断为干燥综合征以及浆细胞型卡斯特曼病,接受了联合化疗和利妥昔单抗治疗,随后接受了18个月的苯丁酸氮芥和泼尼松龙脉冲治疗以及每三个月一次的利妥昔单抗维持治疗。