Department of Developmental Genetics, Max Planck Institute for Heart and Lung Research, Bad Nauheim, 61231, Germany.
Department of Pharmacology, Max Planck Institute for Heart and Lung Research, Bad Nauheim, 61231, Germany.
Nat Commun. 2018 Jul 19;9(1):2815. doi: 10.1038/s41467-018-05043-5.
Tubulogenesis is essential for the formation and function of internal organs. One such organ is the trachea, which allows gas exchange between the external environment and the lungs. However, the cellular and molecular mechanisms underlying tracheal tube development remain poorly understood. Here, we show that the potassium channel KCNJ13 is a critical modulator of tracheal tubulogenesis. We identify Kcnj13 in an ethylnitrosourea forward genetic screen for regulators of mouse respiratory organ development. Kcnj13 mutants exhibit a shorter trachea as well as defective smooth muscle (SM) cell alignment and polarity. KCNJ13 is essential to maintain ion homeostasis in tracheal SM cells, which is required for actin polymerization. This process appears to be mediated, at least in part, through activation of the actin regulator AKT, as pharmacological increase of AKT phosphorylation ameliorates the Kcnj13-mutant trachea phenotypes. These results provide insight into the role of ion homeostasis in cytoskeletal organization during tubulogenesis.
管状形成对于内部器官的形成和功能至关重要。其中一个器官是气管,它允许外部环境和肺部之间的气体交换。然而,气管管腔发育的细胞和分子机制仍知之甚少。在这里,我们表明钾通道 KCNJ13 是气管管状形成的关键调节剂。我们在乙基亚硝脲正向遗传筛选中鉴定出 Kcnj13,用于鉴定调节小鼠呼吸器官发育的调节剂。Kcnj13 突变体表现出较短的气管以及平滑肌 (SM) 细胞排列和极性缺陷。KCNJ13 对于维持气管 SM 细胞中的离子稳态至关重要,这对于肌动蛋白聚合是必需的。这个过程似乎至少部分是通过激活肌动蛋白调节剂 AKT 来介导的,因为 AKT 磷酸化的药理学增加可以改善 Kcnj13 突变体气管表型。这些结果提供了对离子稳态在管状形成过程中细胞骨架组织中的作用的深入了解。