Dayasiri Kavinda, Thadchanamoorthy Vijayakumary
Paediatrics, Base Hospital Mahaoya, Mahaoya, LKA.
Clinical Sciences, Faculty of Health Care Sciences, Eastern University, Batticaloa, LKA.
Cureus. 2021 Jan 26;13(1):e12928. doi: 10.7759/cureus.12928.
PHACE syndrome is a rare disorder of vasculogenesis that occurs during the first trimester of pregnancy. The disorder commonly presents with posterior fossa brain anomalies and coarctation of aorta/arterial anomalies and is predominantly seen in female patients. Herein, we report a male child with PHACE syndrome who had several less common features such as cortical dysplasia, retinal degeneration, and microphthalmia. The diagnosis of PHACE syndrome was confirmed based on revised diagnostic criteria and by the presence of one major criterion and two minor criteria in addition to >5 cm haemangioma. Further, the reported child had atrial septal defect as the only cardiac abnormality, and this has been rarely described in patients with PHACE syndrome.
PHACE综合征是一种罕见的血管生成障碍疾病,发生于妊娠早期。该疾病通常表现为后颅窝脑异常和主动脉缩窄/动脉异常,主要见于女性患者。在此,我们报告一名患有PHACE综合征的男童,他具有一些不太常见的特征,如皮质发育异常、视网膜变性和小眼症。根据修订的诊断标准,并除了有大于5厘米的血管瘤外,还存在一项主要标准和两项次要标准,PHACE综合征的诊断得以确诊。此外,所报告的患儿仅有房间隔缺损这一心脏异常情况,而这在PHACE综合征患者中鲜有描述。