Structural Biology Initiative, CUNY Advanced Science Research Center, New York, New York, USA.
Ph.D. Programs in Biochemistry and Biology, The Graduate Center, CUNY, New York, New York, USA.
Protein Sci. 2021 Jul;30(7):1482-1486. doi: 10.1002/pro.4105. Epub 2021 May 22.
Huntington's disease is caused by a polyglutamine (polyQ) expansion in the huntingtin protein which results in its abnormal aggregation in the nervous system. Huntingtin aggregates are linked to toxicity and neuronal dysfunction, but a comprehensive understanding of the aggregation mechanism in vivo remains elusive. Here, we examine the morphology of polyQ aggregates in Caenorhabditis elegans mechanosensory neurons as a function of age using confocal and fluorescence lifetime imaging microscopy. We find that aggregates in young worms are mostly spherical with homogenous intensity, but as the worm ages aggregates become substantially more heterogeneous. Most prominently, in older worms we observe an apparent core/shell morphology of polyQ assemblies with decreased intensity in the center. The fluorescence lifetime of polyQ is uniform across the aggregate indicating that the dimmed intensity in the assembly center is most likely not due to quenching or changes in local environment, but rather to displacement of fluorescent polyQ from the central region. This apparent core/shell architecture of polyQ aggregates in aging C. elegans neurons contributes to the diverse landscape of polyQ aggregation states implicated in Huntington's disease.
亨廷顿病是由亨廷顿蛋白中的多聚谷氨酰胺(polyQ)扩展引起的,导致其在神经系统中的异常聚集。亨廷顿蛋白聚集与毒性和神经元功能障碍有关,但对体内聚集机制的全面理解仍然难以捉摸。在这里,我们使用共聚焦和荧光寿命成像显微镜检查了秀丽隐杆线虫机械感觉神经元中多聚 Q 聚集体随年龄变化的形态。我们发现,年轻线虫中的聚集体主要是球形的,强度均匀,但随着线虫年龄的增长,聚集体变得更加不均匀。最明显的是,在年老的线虫中,我们观察到聚集体的明显核/壳形态,中心强度降低。多聚 Q 的荧光寿命在整个聚集体中是均匀的,这表明聚集体中心的暗淡强度很可能不是由于猝灭或局部环境变化引起的,而是由于荧光多聚 Q 从中心区域的位移。衰老秀丽隐杆线虫神经元中多聚 Q 聚集体的这种明显的核/壳结构,有助于解释亨廷顿病中多聚 Q 聚集状态的多样性。