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雷特综合征患者因双侧气胸导致急性呼吸功能不全。

Acute respiratory compromise due to bilateral pneumothoraces in a patient with Rett syndrome.

作者信息

Meneely S J, McFadzean J

机构信息

Department of Anaesthetics and Intensive Care Medicine Royal Hospital for Children and Young People Edinburgh UK.

出版信息

Anaesth Rep. 2021 Nov 15;9(2):e12135. doi: 10.1002/anr3.12135. eCollection 2021 Jul-Dec.

Abstract

This is a case of acute respiratory distress in a nine-year-old with severe Rett syndrome who required immediate anaesthetic assistance in the emergency department and during her subsequent hospital stay. Rett syndrome is a rare inherited neurodevelopmental disease that more commonly affects females. It is characterised by a period of normal development up to between six and 18 months of age, followed by a gradual but progressive loss of developmental skills leading to severe cognitive and physical decline. Other features include autistic-type behaviour, oral-motor and autonomic dysfunction and gastrointestinal disturbance. Patients can present for elective surgery for scoliosis correction, ear, nose and throat procedures or placement of a gastrostomy. They can also present acutely, either with an un-associated condition or due to aspiration from a poor gag or swallow. This report highlights the specific risks relevant to anaesthesia in patients with Rett syndrome, especially in considering the association with bilateral apical bullae and pneumothorax which could impact on the ventilation strategy.

摘要

这是一例9岁重度雷特综合征患儿急性呼吸窘迫的病例,该患儿在急诊科及随后住院期间均需要立即给予麻醉辅助。雷特综合征是一种罕见的遗传性神经发育疾病,更常见于女性。其特征是在6至18个月龄之前发育正常,随后逐渐但渐进性地丧失发育技能,导致严重的认知和身体衰退。其他特征包括自闭症样行为、口腔运动和自主神经功能障碍以及胃肠道紊乱。患者可能因脊柱侧弯矫正、耳鼻喉手术或胃造口术而接受择期手术。他们也可能因无关疾病或由于吞咽反射差或吞咽功能不佳导致误吸而急性发病。本报告强调了雷特综合征患者麻醉相关的特定风险,尤其是考虑到与双侧肺尖大疱和气胸的关联可能会影响通气策略。

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本文引用的文献

1
Evaluation of QTc in Rett syndrome: Correlation with age, severity, and genotype.
Am J Med Genet A. 2017 Jun;173(6):1495-1501. doi: 10.1002/ajmg.a.38191. Epub 2017 Apr 10.
2
Subclinical inflammatory status in Rett syndrome.
Mediators Inflamm. 2014;2014:480980. doi: 10.1155/2014/480980. Epub 2014 Jan 6.
3
Cardiorespiratory challenges in Rett's syndrome.
Lancet. 2008 Jun 14;371(9629):1981-3. doi: 10.1016/S0140-6736(08)60849-1.
4
The story of Rett syndrome: from clinic to neurobiology.
Neuron. 2007 Nov 8;56(3):422-37. doi: 10.1016/j.neuron.2007.10.001.
7
Review of Rett syndrome.
J Neuropathol Exp Neurol. 1997 Aug;56(8):843-9. doi: 10.1097/00005072-199708000-00001.
8
Rett syndrome: clinical peculiarities and biological mysteries.
Acta Paediatr. 1995 Sep;84(9):971-6. doi: 10.1111/j.1651-2227.1995.tb13809.x.

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