Department of Internal Medicine, Al-Quds University Faculty of Medicine, East Jerusalem, Palestinian Territory, Occupied.
Department of Internal Medicine, Hadassah University Hospital, Jerusalem, Israel.
Am J Case Rep. 2022 Feb 27;23:e935636. doi: 10.12659/AJCR.935636.
BACKGROUND Acute hemorrhagic leukoencephalitis (AHLE) is a very rare fulminant post-infectious demyelinating disease of the CNS. We report an atypical presentation of AHLE involving unique brain areas 2 weeks following a viral upper-respiratory tract infection (URTI). Early diagnosis and proper management improve the prognosis of this disease, and AHLE can have a very poor prognosis and high mortality rate. CASE REPORT A 52-year-old male patient was referred for deteriorating consciousness 2 weeks after a viral URTI. An initial brain CT scan showed multiple patchy bilateral and diffuse hypodense areas including the cerebellar, occipital, parietal, and frontal lobes. The diagnostic workup also included CSF analysis and MRI of the brain, which revealed multiple areas of hemorrhagic involvement. Management included broad-spectrum antibiotics, acyclovir, mannitol, steroids, and plasmapheresis. On the fifth day of admission, brain CT showed severe diffuse edema and brain herniation. Unfortunately, despite prompt aggressive treatment measures, within 48 hours the patient died due to centrally-mediated hemodynamic instability. CONCLUSIONS We report a rare case of AHLE with a unique presentation and extensive unusual involvement of regions of periventricular and subcortical white matter, cerebellum, and midbrain. Early diagnosis along with appropriate management measures and intensive care can help decrease morbidity and mortality; therefore, prompt referral and high-level care should be sought for all patients who present with acute deteriorating consciousness. We hope that this report can help future studies to better characterize this rare disease and provide further guidance regarding prognosis and management.
急性出血性白质脑炎(AHLE)是一种非常罕见的暴发性中枢神经系统感染后脱髓鞘疾病。我们报告了一例涉及独特脑区的 AHLE 不典型表现,该患者在病毒上呼吸道感染(URTI)后 2 周出现该疾病。早期诊断和适当的治疗可以改善这种疾病的预后,而 AHLE 预后非常差,死亡率高。
一名 52 岁男性患者在病毒性 URTI 后 2 周因意识恶化而被转介。初始脑 CT 扫描显示双侧和弥漫性多个斑块状低密区,包括小脑、枕叶、顶叶和额叶。诊断工作还包括脑脊液分析和脑 MRI,显示多处出血性病变。治疗包括广谱抗生素、阿昔洛韦、甘露醇、类固醇和血浆置换。入院第 5 天,脑 CT 显示严重弥漫性水肿和脑疝。不幸的是,尽管采取了迅速积极的治疗措施,但在 48 小时内,患者因中枢介导的血流动力学不稳定而死亡。
我们报告了一例罕见的 AHLE 病例,具有独特的表现和广泛的脑室周围和皮质下白质、小脑和中脑的异常受累。早期诊断和适当的治疗措施以及重症监护可以降低发病率和死亡率;因此,所有出现急性意识恶化的患者都应及时转诊并接受高级别的治疗。我们希望本报告可以帮助未来的研究更好地描述这种罕见疾病,并为预后和治疗提供进一步的指导。