Pieroni Maurizio, Zocchi Chiara, Ciabatti Michele
Department of Experimental and Clinical Medicine, University of Florence, Largo Brambilla 3, 50135 Florence, Italy.
Careggi University Hospital, Largo Brambilla 3, 50135 Florence, Italy.
Eur Heart J Suppl. 2025 Feb 19;27(Suppl 1):i51-i55. doi: 10.1093/eurheartjsupp/suae104. eCollection 2025 Feb.
Fabry disease is an X-linked lysosomal storage disorder caused by deficient activity of the enzyme α-galactosidase A, leading to the accumulation of globotriaosylceramide in various tissues, including the heart. Cardiac involvement is a prominent feature and a major cause of morbidity and mortality in Fabry disease, manifesting as left ventricular hypertrophy, myocardial ischaemia, heart failure, and arrhythmias. Secondary mechanisms, triggered by lysosomal storage, contribute to myocardial damage, in particular, myocardial inflammation. Early cardiac involvement can be subtle, but with disease progression, it becomes a major determinant of morbidity and mortality. Recent progresses in diagnostic techniques, such as advanced cardiac magnetic resonance imaging with T1 and T2 mapping, have improved early detection of Fabry-related cardiac disease. Enzyme replacement therapy and newer treatments like chaperone therapy have shown potential in managing cardiac manifestations when initiated early, while the progression of cardiac involvement may be difficult to halt in patients diagnosed late in the disease course. Gene therapy and substrate reduction therapy are emerging treatment modalities that hold promise but require further clinical evaluation. The limited efficacy of available therapies and the variability of cardiac response to treatment represent main unresolved issues, together with challenges in monitoring disease progression, and the need for additional therapeutic strategies targeting secondary mechanisms. Unmet needs in clinical practice include the identification of disease-specific and cardiac-specific biomarkers for early detection, staging, and monitoring cardiac damage. Similarly, strategies for prognostic stratification and better prevention of cardiovascular complications are essential to improve the care of these patients.
法布里病是一种X连锁溶酶体贮积症,由α-半乳糖苷酶A活性缺乏引起,导致包括心脏在内的各种组织中球三糖神经酰胺蓄积。心脏受累是法布里病的一个突出特征,也是发病和死亡的主要原因,表现为左心室肥厚、心肌缺血、心力衰竭和心律失常。由溶酶体贮积引发的继发机制会导致心肌损伤,尤其是心肌炎症。早期心脏受累可能不明显,但随着疾病进展,它会成为发病和死亡的主要决定因素。诊断技术的最新进展,如采用T1和T2映射的先进心脏磁共振成像,已改善了法布里相关心脏疾病的早期检测。酶替代疗法和伴侣疗法等新疗法在早期启动时已显示出治疗心脏表现的潜力,而在疾病病程后期诊断的患者中,心脏受累的进展可能难以阻止。基因疗法和底物减少疗法是新兴的治疗方式,具有前景,但需要进一步的临床评估。现有疗法的疗效有限以及心脏对治疗反应的变异性是主要未解决的问题,同时在监测疾病进展方面存在挑战,并且需要针对继发机制的额外治疗策略。临床实践中未满足的需求包括识别用于早期检测、分期和监测心脏损伤的疾病特异性和心脏特异性生物标志物。同样,预后分层和更好地预防心血管并发症的策略对于改善这些患者的护理至关重要。