Kaabi Noor Al, Camacho Encarna, Orchanian-Cheff Ani, Silano Vanessa, McGillis Laura, Truong Wing Ting, Reid W Darlene, Chow Chung-Wai, Ryan Clodagh M, Slepian Maxwell, Santa Mina Daniel, Clarke Hance, Mittal Nimish, Rozenberg Dmitry
Division of Respirology, University Health Network, Toronto, ON M5G 2C4, Canada.
Temerty Faculty of Medicine, University of Toronto, Toronto, ON M5R 0A3, Canada.
J Clin Med. 2025 Jun 11;14(12):4126. doi: 10.3390/jcm14124126.
Ehlers-Danlos Syndromes (EDS) and Generalized Hypermobility Spectrum disorders (G-HSD) are a group of genetic, connective multi-systemic disorders that can affect the musculoskeletal, gastrointestinal, cardiovascular, and respiratory systems. Respiratory manifestations in EDS/G-HSD can contribute to decrements in health-related quality of life (HRQL); however, these relationships have not been previously characterized. We aimed to review the association of respiratory manifestations with the physical, psychological, and social domains of HRQL in EDS/G-HSD. A comprehensive search was conducted using Ovid Medline, Embase, and CINAHL with the following terms: "Ehlers-Danlos Syndrome", "Hypermobility Spectrum Disorders", and "Quality of Life". Selected studies in English that investigated the relationship between respiratory manifestations and HRQL domains in EDS/G-HSD were included in this narrative review from inception to March 2024. Twelve studies described the physical, psychological, or social domains of HRQL relating to respiratory manifestations. Dyspnea, wheezing, and expiratory flow limitations were associated with limitations in physical function and exercise intolerance. Respiratory manifestations were associated with increased fatigue, pain, anxiety, kinesiophobia, and deconditioning. This review highlights the consequences that respiratory manifestations have on the physical domains of HRQL, through limitations on physical activity and exercise. Future studies should aim to identify the impact that respiratory manifestations have on the psychosocial domains of HRQL and develop disease-specific patient-reported measures to evaluate these relationships.
埃勒斯-当洛综合征(EDS)和全身性关节过度活动谱系障碍(G-HSD)是一组遗传性、累及多系统的结缔组织疾病,可影响肌肉骨骼、胃肠道、心血管和呼吸系统。EDS/G-HSD中的呼吸系统表现会导致健康相关生活质量(HRQL)下降;然而,这些关系此前尚未得到描述。我们旨在综述EDS/G-HSD中呼吸系统表现与HRQL的身体、心理和社会领域之间的关联。使用Ovid Medline、Embase和CINAHL进行了全面检索,检索词如下:“埃勒斯-当洛综合征”、“关节过度活动谱系障碍”和“生活质量”。本叙述性综述纳入了从开始到2024年3月期间发表的、用英文撰写的、研究EDS/G-HSD中呼吸系统表现与HRQL领域之间关系的选定研究。12项研究描述了与呼吸系统表现相关的HRQL的身体、心理或社会领域。呼吸困难、喘息和呼气流量受限与身体功能受限和运动不耐受有关。呼吸系统表现与疲劳、疼痛、焦虑、运动恐惧和身体机能下降增加有关。本综述强调了呼吸系统表现通过限制身体活动和运动对HRQL身体领域产生的影响。未来的研究应旨在确定呼吸系统表现对HRQL心理社会领域的影响,并制定针对特定疾病的患者报告测量方法来评估这些关系。