Kao Hsiao-Wen, Chang Hung, Kuo Ming-Chung, Wu Jin-Hou, Huang Ying-Jung, Huang Ting-Yu, Lin Tung-Huei, Shih Lee-Yung
Division of Hematology-Oncology, Chang Gung Memorial Hospital at Linkou, Taoyuan, Taiwan.
School of Medicine, Chang Gung University, Taoyuan, Taiwan.
Cancer. 2025 Aug 15;131(16):e70048. doi: 10.1002/cncr.70048.
Clonal evolution drives progression of myeloproliferative neoplasms (MPN) from chronic phase (CP) to blastic phase (BP).
Targeted next-generation sequencing of 46 paired MPN-CP/BP samples was performed to assess clonal evolution through variant allele frequency changes.
The median time from MPN-CP to BP was 6.9 (range 0.3-27.8) years. In MPN-CP, driver mutation frequency was 98% (JAK2-V617F 67%, CALR 28%, MPL 2%), decreased to 78% in BP due to JAK2-V617F loss, with all CALR mutations preserved. Total mutation numbers increased during BP progression (median 2 in CP vs. 3 in BP, p < .001). Epigenetic mutations (TET2 24%, DNMT3A 17%, ASXL1 15%, EZH2 11%) were common in CP and persisted or expanded in BP, with occasional acquisition of ASXL1 (p = .074), EZH2, and IDH1/2 mutations. Spliceosome mutations rose from 26% to 39% and transcription-related mutations from 13% to 33%. RUNX1, TP53, and most signaling gene mutations emerged predominantly in BP. JAK2-V617F, often preceded by TET2, ASXL1, DNMT3A, or EZH2 mutations, persisted or was replaced by other subclones in BP. Female and JAK2-V617F loss were linked to shorter time to BP and poorer survival from CP. Survival after BP was lower in patients acquiring signaling mutations but improved with hematopoietic stem cell transplantation.
MPN transformation involves complex clonal evolution, with frequent clonal hematopoiesis-related mutations preceding driver mutations, preserved CALR, acquisition of TP53, RUNX1 and signaling mutations, and JAK2-V617F loss linked to poorer survival during BP transformation, which may influence therapeutic decisions.
克隆进化驱动骨髓增殖性肿瘤(MPN)从慢性期(CP)进展为急变期(BP)。
对46对MPN-CP/BP样本进行靶向二代测序,通过变异等位基因频率变化评估克隆进化。
从MPN-CP到BP的中位时间为6.9(范围0.3 - 27.8)年。在MPN-CP中,驱动基因突变频率为98%(JAK2-V617F 67%,CALR 28%,MPL 2%),由于JAK2-V617F缺失,在BP中降至78%,而所有CALR突变均保留。在BP进展过程中,总突变数增加(CP中位值为2,BP为3,p <.001)。表观遗传突变(TET2 24%,DNMT3A 17%,ASXL1 15%,EZH2 11%)在CP中常见,在BP中持续存在或扩展,偶尔获得ASXL1(p = 0.074)、EZH2和IDH1/2突变。剪接体突变从26%升至39%,转录相关突变从13%升至33%。RUNX1、TP53和大多数信号基因突变主要出现在BP中。JAK2-V617F通常先于TET2、ASXL1、DNMT3A或EZH2突变出现,在BP中持续存在或被其他亚克隆取代。女性和JAK2-V617F缺失与从CP到BP的时间较短及较差的生存率相关。获得信号基因突变的患者在BP后的生存率较低,但造血干细胞移植可改善生存率。
MPN转化涉及复杂的克隆进化,克隆造血相关突变频繁先于驱动基因突变出现,CALR保留,获得TP53、RUNX1和信号基因突变,以及JAK2-V617F缺失与BP转化期间较差的生存率相关,这可能影响治疗决策。