Ibrahimi Ahmed, Abiir Youssef, Gounni Yassine, Kallat Adil, Boualaoui Imad, El Abidi Hamza
Urology A Department, University Hospital ibn Sina, Rabat, Morocco.
Provincial Hospital Center of Azilal, Azilal, Morocco.
Int J Surg Case Rep. 2025 Oct;135:111780. doi: 10.1016/j.ijscr.2025.111780. Epub 2025 Aug 6.
Hair-thread tourniquet syndrome (HTTS) represents a rare entity that can result in significant morbidity if not promptly identified and treated. Characterized by constriction of appendages by hair or thread, resulting in vascular compromise, ischemia, and potential tissue necrosis.
We present the case of a 9-year-old circumcised male who developed penile HTTS, manifesting as severe edema, erythema, partial ischemia, and near-complete urethral transection. The constricting thread was excised emergently, and termino-terminal urethral anastomosis was performed. Multilayered reconstruction, including coverage with a dartos flap, was employed. The postoperative recovery was unremarkable, with imaging confirming entire urethral continuity and voiding symptoms resolved.
Early identification is critical since it can resemble infections and lead to serious consequences. Conservative treatment options include depilatory creams and mechanical removal, as well as surgical treatment, such as phased urethral restoration. In severe situations, microsurgical replantation is necessary to restore vascular integrity, nerve function, and urethral alignment.
This example demonstrates the possibility of one-stage repair in complicated cases and the importance of keeping a high degree of suspicion for HTTS in individuals presenting with unexplained penile edema.
毛发-丝线束带综合征(HTTS)是一种罕见病症,若未及时识别和治疗,可导致严重发病情况。其特征为毛发或丝线对附属器造成压迫,进而导致血管受压、缺血以及潜在的组织坏死。
我们报告一例9岁行包皮环切术的男性发生阴茎HTTS的病例,表现为严重水肿、红斑、部分缺血以及近乎完全的尿道横断。紧急切除束带丝线,并进行端端尿道吻合术。采用了包括肉膜瓣覆盖的多层重建术。术后恢复情况良好,影像学检查证实尿道完全连续,排尿症状得以解决。
早期识别至关重要,因为它可能类似感染并导致严重后果。保守治疗选择包括脱毛膏和机械去除,以及手术治疗,如分期尿道修复。在严重情况下,显微外科再植术对于恢复血管完整性、神经功能和尿道对合是必要的。
该病例表明复杂病例进行一期修复的可能性,以及对出现不明原因阴茎水肿的个体高度怀疑HTTS的重要性。