Shillito P, Molenaar P C, Vincent A, Leys K, Zheng W, van den Berg R J, Plomp J J, van Kempen G T, Chauplannaz G, Wintzen A R
Neurosciences Group, Institute of Molecular Medicine, University of Oxford, United Kingdom.
Ann Neurol. 1995 Nov;38(5):714-22. doi: 10.1002/ana.410380505.
Acquired neuromyotonia is characterized by hyperexcitability of motor nerves leading to muscle twitching, cramps, and weakness. The symptoms may improve following plasma exchange, and injection of immunoglobulin G (IgG) from 1 neuromyotonia patient into mice increased the resistance of neuromuscular transmission to d-tubocurarine. Here we examine nerves and muscle in vitro from mice injected with plasma or purified IgG from 6 neuromyotonia patients or pooled control subjects, and cultured dorsal root ganglion cells after treatment with IgG. Three of the patients had antibodies against human voltage-gated potassium channels labeled with 125I-alpha-dendrotoxin. The quantal release of acetylcholine (quantal content) at end-plates in diaphragms from mice treated with neuromyotonia IgG preparations was increased by 21% relative to control values (p = 0.0053). With one IgG preparation, the duration of the superficial peroneal nerve compound action currents was increased by 93%. The dorsal root ganglion cells treated with this IgG showed a marked increase in repetitive firing of action potentials. All effects were similar to those obtained with aminopyridines. We conclude that at least some patients with acquired neuromyotonia have antibodies directed against aminopyridine- or alpha-dendrotoxin-sensitive K+ channels in motor and sensory neurons, and they are likely to be implicated in the disease process.
获得性神经性肌强直的特征是运动神经兴奋性过高,导致肌肉抽搐、痉挛和无力。血浆置换后症状可能改善,将一名神经性肌强直患者的免疫球蛋白G(IgG)注射到小鼠体内可增加神经肌肉传递对d - 筒箭毒碱的抵抗力。在此,我们检测了注射了6名神经性肌强直患者或混合对照受试者的血浆或纯化IgG的小鼠的体外神经和肌肉,以及用IgG处理后的培养背根神经节细胞。其中三名患者具有针对用125I-α-树眼镜蛇毒素标记的人电压门控钾通道的抗体。相对于对照值,用神经性肌强直IgG制剂处理的小鼠膈肌终板处乙酰胆碱的量子释放量(量子含量)增加了21%(p = 0.0053)。使用一种IgG制剂时,腓浅神经复合动作电流的持续时间增加了93%。用这种IgG处理的背根神经节细胞动作电位的重复发放显著增加。所有效应均与使用氨基吡啶所获得的效应相似。我们得出结论,至少部分获得性神经性肌强直患者具有针对运动和感觉神经元中氨基吡啶或α-树眼镜蛇毒素敏感的钾通道的抗体,并且它们可能与疾病过程有关。