Kersten Hannah M, Roxburgh Richard H, Danesh-Meyer Helen V, Hutchinson David O
Department of Ophthalmology, University of Auckland, Auckland, New Zealand.
Department of Neurology, Auckland City Hospital, 2 Park Road, Auckland 1023, New Zealand.
J Clin Neurosci. 2016 Sep;31:199-201. doi: 10.1016/j.jocn.2016.02.015. Epub 2016 Apr 1.
Type 1 sialidosis is a metabolic storage disorder characterised by the accumulation of sialylated oligosaccharides. The condition is also known as macular cherry-red spot and myoclonus syndrome due to the characteristic macular appearance in affected individuals. This case outlines the presentation of a patient with type 1 sialidosis, including ophthalmological assessment with retinal photography and spectral domain optical coherence tomography (OCT). OCT scans showed thickening of the perimacular and peripapillary retinal nerve fibre layer, thought to be due to the abnormal accumulation of metabolic products. The cherry-red spot appearance is due to the normal appearing macula being seen in contrast to the abnormally pale surrounding, thickened retinal nerve fibre layer.
1型唾液酸沉积症是一种代谢性贮积病,其特征为唾液酸化寡糖的蓄积。由于受影响个体具有特征性的黄斑外观,该病症也被称为黄斑樱桃红斑和肌阵挛综合征。本病例概述了一名1型唾液酸沉积症患者的表现,包括使用视网膜摄影和光谱域光学相干断层扫描(OCT)进行眼科评估。OCT扫描显示黄斑周围和视乳头周围视网膜神经纤维层增厚,认为这是由于代谢产物异常蓄积所致。樱桃红斑外观是由于正常的黄斑与周围异常苍白、增厚的视网膜神经纤维层形成对比所致。