Alif N, Hess K, Straczek J, Sebbar S, N'Bou A, Nabet P, Dousset B
Laboratory of Cellular and Molecular Biology, Ibnou Zohr University School of Sciences, Agadir, Morocco.
Ann Hum Genet. 1999 Jan;63(Pt 1):9-16. doi: 10.1046/j.1469-1809.1999.6310009.x.
A group of 13 Moroccan patients with MPS I and their families, including three siblings and twin siblings, was screened for mutations of the alpha-L-iduronidase gene using fluorescence-assisted mismatch analysis (FAMA) and cycle sequencing of PCR products. The P533R mutation, which is rare in Europeans, was identified in 92% of mutant alleles (24/26). This is the highest frequency of this mutation detected in patients with Hurler syndrome. None of the patients carried the W402X or Q70X alleles, the most common MPS I mutations in Europeans. These results suggest that the P533R mutation constitutes the genetic lesion which results in MPS I in people of Moroccan descent and provides yet more evidence for the uneven geographical distribution of mutations in MPS I.
一组13名患有黏多糖贮积症I型的摩洛哥患者及其家属,包括三对兄弟姐妹和一对双胞胎,采用荧光辅助错配分析(FAMA)和PCR产物循环测序技术,对α-L-艾杜糖醛酸酶基因的突变情况进行了筛查。在欧洲人中罕见的P533R突变,在92%的突变等位基因(24/26)中被检测到。这是在Hurler综合征患者中检测到的该突变的最高频率。这些患者均未携带欧洲人中最常见的MPS I突变W402X或Q70X等位基因。这些结果表明,P533R突变是导致摩洛哥裔人群患MPS I的遗传损伤,并且为MPS I突变的地理分布不均提供了更多证据。