Fan H C, Hung C H, Juan C J, Hsu M L, Huang C F, Tsai Y G, Harn H J, Yuh Y S, Cheng S N
Department of Pediatrics, Tri-Service General Hospital, Taipei, Taiwan.
Acta Paediatr Taiwan. 2000 Jul-Aug;41(4):214-7.
Subglottic hemangioma (SGH) is a benign neoplasm that may cause severe and life-threatening respiratory obstruction in infants. However, patients usually present with inspiratory stridor in the first few months of life and may be mistakenly diagnosed as recurrent or persistent croup. Definitive diagnosis is made by image studies, endoscopic examination and biopsy or all. We report a 2-month-old female infant of SGH with initial clinical manifestations of dyspnea and inspiratory stridor co-existing with cutaneous and cerebellar hemangiomas. Clinicians must be alert the possibility of SGH when associated with cutaneous hemangioma. This patient has received oral steroid treatment for more than two months with improvement of the airway obstruction. Although purplish patch lesions over left side of face, eyelid, cheek, and peri-oral regions regressed, the size of the SGH on the followed MRI was slightly enlarged. The diagnosis and various treatments of SGH are discussed and reviewed in this paper.
声门下血管瘤(SGH)是一种良性肿瘤,可导致婴儿出现严重且危及生命的呼吸道梗阻。然而,患者通常在出生后的头几个月出现吸气性喘鸣,可能被误诊为复发性或持续性喉炎。通过影像学检查、内镜检查和活检或综合这些方法进行明确诊断。我们报告一例2个月大的SGH女婴,其初始临床表现为呼吸困难和吸气性喘鸣,同时伴有皮肤和小脑血管瘤。当与皮肤血管瘤相关时,临床医生必须警惕SGH的可能性。该患者接受口服类固醇治疗两个多月,气道梗阻有所改善。尽管左侧面部、眼睑、脸颊和口周区域的紫色斑块病变有所消退,但后续MRI显示SGH的大小略有增大。本文对SGH的诊断和各种治疗方法进行了讨论和综述。