Zimonjic D B, Pollock J L, Westervelt P, Popescu N C, Ley T J
Molecular Cytogenetics Section, Laboratory of Experimental Carcinogenesis, National Cancer Institute, Bethesda, MD 20892, USA.
Proc Natl Acad Sci U S A. 2000 Nov 21;97(24):13306-11. doi: 10.1073/pnas.97.24.13306.
We previously generated a transgenic mouse model for acute promyelocytic leukemia (APL) by expressing the promyelocytic leukemia (PML)-retinoic acid receptor (RARalpha) cDNA in early myeloid cells. This fusion protein causes a myeloproliferative disease in 100% of animals, but only 15-20% of the animals develop acute leukemia after a long latency period (6-13 months). PML-RARalpha is therefore necessary, but not sufficient, for APL development. The coexpression of a reciprocal form of the fusion, RARalpha-PML, increased the likelihood of APL development (55-60%), but did not shorten latency. Together, these results suggested that additional genetic events are required for the development of APL. We therefore evaluated the splenic tumor cells from 18 transgenic mice with APL for evidence of secondary genetic events, by using spectral karyotyping analysis. Interstitial or terminal deletions of the distal region of one copy of chromosome 2 [del(2)] were found in 1/5 tumors expressing PML-RARalpha, but in 11/13 tumors expressing both PML-RARalpha and RARalpha-PML (P < 0.05). Leukemic cells that contained a deletion on chromosome 2 often contained additional chromosomal gains (especially of 15), chromosomal losses (especially of 11 or X/Y), or were tetraploid (P </= 0.001). These changes did not commonly occur in nontransgenic littermates, nor in aged transgenic mice that did not develop APL. These results suggest that expression of RARalpha-PML increases the likelihood of chromosome 2 deletions in APL cells. Deletion 2 appears to predispose APL cells to further chromosomal instability, which may lead to the acquisition of additional changes that provide an advantage to the transformed cells.
我们之前通过在早期髓系细胞中表达早幼粒细胞白血病(PML)-维甲酸受体(RARα)cDNA,生成了一种急性早幼粒细胞白血病(APL)的转基因小鼠模型。这种融合蛋白在100%的动物中引发骨髓增殖性疾病,但只有15 - 20%的动物在长时间潜伏期(6 - 13个月)后发展为急性白血病。因此,PML - RARα对于APL的发生是必要的,但并不充分。融合蛋白的反向形式RARα - PML的共表达增加了APL发生的可能性(55 - 60%),但并未缩短潜伏期。这些结果共同表明,APL的发生还需要其他遗传事件。因此,我们通过光谱核型分析评估了18只患有APL的转基因小鼠的脾肿瘤细胞,以寻找继发性遗传事件的证据。在表达PML - RARα的1/5肿瘤中发现了2号染色体一个拷贝远端区域的间质或末端缺失[del(2)],但在同时表达PML - RARα和RARα - PML的11/13肿瘤中发现了这种缺失(P < 0.05)。含有2号染色体缺失的白血病细胞通常还伴有其他染色体增加(尤其是15号染色体)、染色体丢失(尤其是11号或X/Y染色体),或者是四倍体(P≤0.001)。这些变化在非转基因同窝小鼠中以及未发生APL的老年转基因小鼠中并不常见。这些结果表明,RARα - PML的表达增加了APL细胞中2号染色体缺失的可能性。2号染色体缺失似乎使APL细胞更容易发生进一步的染色体不稳定,这可能导致获得其他变化,从而为转化细胞提供优势。