Hedera P, Gorski J L
Department of Pediatrics, Division of Pediatric Genetics, University of Michigan, Ann Arbor, Michigan 48109, USA.
Am J Med Genet. 2001 Jun 15;101(2):142-5. doi: 10.1002/ajmg.1338.
Here we report two brothers with retinitis pigmentosa, growth hormone deficiency, and acromelic skeletal dysplasia. We propose that their clinical picture is consistent with RHYNS syndrome (retinitis pigmentosa, hypopituitarism, nephronophthisis, and skeletal dysplasia) and that they represent the first instance of a familial occurrence of this syndrome. The presence of RHYNS in two siblings supports an autosomal recessive mode of inheritance; however, since all four known cases were male, an X-linked mode of inheritance cannot be excluded. The combination of clinical features found in these affected males is unique and supports the existence of RHYNS syndrome as a separate and distinct entity.
在此,我们报告了两名患有色素性视网膜炎、生长激素缺乏症和肢端短小骨骼发育异常的兄弟。我们认为他们的临床症状符合RHYNS综合征(色素性视网膜炎、垂体功能减退、肾单位肾痨和骨骼发育异常),且他们代表了该综合征家族性发病的首例。两名兄弟姐妹均患有RHYNS综合征,这支持了常染色体隐性遗传模式;然而,由于所有已知的4个病例均为男性,也不能排除X连锁遗传模式。在这些受影响男性中发现的临床特征组合是独特 的,支持了RHYNS综合征作为一个独立且独特的病症存在。