Dippel E, Poenitz N, Klemke C D, Orfanos C E, Goerdt S
Department of Dermatology, University Medical Center Benjamin Franklin, Free University of Berlin, Germany.
Dermatology. 2002;204(1):12-6. doi: 10.1159/000051803.
Lymphocytic infiltration of the skin (Jessner and Kanof) is a T cell pseudolymphoma characterized by the occurrence of recurrent asymptomatic papules and plaques and by a coat-sleeve-like perivascular lymphoid infiltrate. Rarely, familial cases have been reported.
Our study was performed to address the question of a genetic predisposition in a case of familial lymphocytic infiltration by histochemical and molecular analysis.
We report on 3 brothers with typical clinical and histological features of Jessner's lymphocytic infiltration of the skin. Immunohistochemical analysis revealed a mixed lymphocytic infiltrate with a predominance of CD8+ T cells in all 3 patients. Molecular determination of T cell clonality by PCR-based GeneScan analysis of the T cell receptor (TCR)-gamma-chain showed oligoclonal, pseudomonoclonal or polyclonal TCR-gamma rearrangement patterns in lesional skin and in peripheral blood of all 3 brothers, while no common TCR idiotype was detected.
Inherited deviations in TCR usage seem unlikely as a special cause of familial Jessner's lymphocytic infiltration of the skin; lack of clonality furthermore supports the notion that this variant of the disease is as true a pseudo-T-cell lymphoma as are the spontaneous cases.
皮肤淋巴细胞浸润症(杰斯纳和卡诺夫病)是一种T细胞假性淋巴瘤,其特征为反复出现无症状丘疹和斑块,以及出现袖口样血管周围淋巴细胞浸润。家族性病例报道罕见。
我们的研究旨在通过组织化学和分子分析,探讨家族性淋巴细胞浸润病例中的遗传易感性问题。
我们报道了3例具有杰斯纳皮肤淋巴细胞浸润典型临床和组织学特征的兄弟。免疫组织化学分析显示,所有3例患者均有混合淋巴细胞浸润,且以CD8+T细胞为主。通过基于聚合酶链反应(PCR)的基因扫描分析T细胞受体(TCR)-γ链来确定T细胞克隆性,结果显示所有3例兄弟的皮损皮肤和外周血中均有寡克隆、假单克隆或多克隆TCR-γ重排模式,而未检测到共同的TCR独特型。
TCR使用的遗传偏差似乎不太可能是家族性杰斯纳皮肤淋巴细胞浸润的特殊原因;缺乏克隆性进一步支持了这样一种观点,即该疾病变体与散发性病例一样,是真正的假性T细胞淋巴瘤。