Horwitz Edwin M, Gordon Patricia L, Koo Winston K K, Marx Jeffrey C, Neel Michael D, McNall Rene Y, Muul Linda, Hofmann Ted
Transplantation and Gene Therapy Program, St. Jude Children's Research Hospital, 332 North Lauderdale, Memphis, TN 38105, USA.
Proc Natl Acad Sci U S A. 2002 Jun 25;99(13):8932-7. doi: 10.1073/pnas.132252399.
Treatment with isolated allogeneic mesenchymal cells has the potential to enhance the therapeutic effects of conventional bone marrow transplantation in patients with genetic disorders affecting mesenchymal tissues, including bone, cartilage, and muscle. To demonstrate the feasibility of mesenchymal cell therapy and to gain insight into the transplant biology of these cells, we used gene-marked, donor marrow-derived mesenchymal cells to treat six children who had undergone standard bone marrow transplantation for severe osteogenesis imperfecta. Each child received two infusions of the allogeneic cells. Five of six patients showed engraftment in one or more sites, including bone, skin, and marrow stroma, and had an acceleration of growth velocity during the first 6 mo postinfusion. This improvement ranged from 60% to 94% (median, 70%) of the predicted median values for age- and sex-matched unaffected children, compared with 0% to 40% (median, 20%) over the 6 mo immediately preceding the infusions. There was no clinically significant toxicity except for an urticarial rash in one patient just after the second infusion. Failure to detect engraftment of cells expressing the neomycin phosphotransferase marker gene suggested the potential for immune attack against therapeutic cells expressing a foreign protein. Thus, allogeneic mesenchymal cells offer feasible posttransplantation therapy for osteogenesis imperfecta and likely other disorders originating in mesenchymal precursors.
用分离的同种异体间充质细胞进行治疗,有可能增强传统骨髓移植对患有影响间充质组织(包括骨骼、软骨和肌肉)的遗传性疾病患者的治疗效果。为了证明间充质细胞治疗的可行性并深入了解这些细胞的移植生物学特性,我们使用基因标记的供体骨髓来源的间充质细胞治疗了6名因严重成骨不全症接受标准骨髓移植的儿童。每个儿童接受了两次同种异体细胞输注。6名患者中有5名在一个或多个部位(包括骨骼、皮肤和骨髓基质)出现植入,并在输注后的前6个月内生长速度加快。与输注前6个月0%至40%(中位数为20%)相比,这种改善幅度为年龄和性别匹配的未受影响儿童预测中位数的60%至94%(中位数为70%)。除了一名患者在第二次输注后立即出现荨麻疹皮疹外,没有临床上显著的毒性。未能检测到表达新霉素磷酸转移酶标记基因的细胞植入,提示可能存在针对表达外源蛋白的治疗细胞的免疫攻击。因此,同种异体间充质细胞为成骨不全症以及可能起源于间充质前体细胞的其他疾病提供了可行的移植后治疗方法。