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II型毛发鼻指综合征(朗格-吉迪恩综合征)。

Trichorhinophalangeal syndrome, type II (Langer-Giedion syndrome).

作者信息

Shin H T, Chang M W

机构信息

The Ronald O. Perelman Department of Dermatology, New York University Medical Center, New York, New York, USA.

出版信息

Dermatol Online J. 2001 Dec;7(2):8.

Abstract

Trichorhinophalangeal syndrome (TRPS) is characterized by its unique facial features and skeletal abnormalities. A bulbous, pear-shaped nose, elongated philtrum, sparse hair, cone-shaped epiphyses and mild growth retardation are found in both type I (TRPSI) and type II (TRPSII). TRPSII can be distinguished from TRPSI when multiple exostoses or redundant skin are present. While TRPSI is inherited in an autosomal dominant fashion, most cases of TRPSII are sporadic although there are a few cases which are familial. The following is a case report of TRPSII with incomplete penetrance in the index case and exostoses and growth retardation in the patient's two siblings.

摘要

毛发鼻指综合征(TRPS)的特征在于其独特的面部特征和骨骼异常。I型(TRPSI)和II型(TRPSII)均有球根状、梨形鼻、人中延长、毛发稀疏、骨骺呈锥形以及轻度生长发育迟缓的表现。当存在多个外生骨疣或多余皮肤时,TRPSII可与TRPSI相鉴别。TRPSI以常染色体显性方式遗传,而TRPSII的大多数病例为散发性,不过也有少数家族性病例。以下是一例TRPSII的病例报告,先证者存在不完全外显,且患者的两个兄弟姐妹有外生骨疣和生长发育迟缓的情况。

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引用本文的文献

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