Forrester Mathias B, Merz Ruth D
Hawaii Birth Defects Program, Honolulu, Hawaii 96817-5157, USA.
Am J Med Genet A. 2003 Jun 15;119A(3):305-10. doi: 10.1002/ajmg.a.20150.
Sex chromosome abnormalities such as Turner syndrome, Klinefelter syndrome, triple X syndrome, and 47,XYY can be prenatally diagnosed and electively terminated. This investigation examined the pattern of pregnancy outcome of prenatally and postnatally diagnosed sex chromosome abnormalities in Hawaii during 1986-1999 and calculated prenatal diagnosis and subsequent elective termination rates for various factors. Data were obtained from a statewide population-based birth defects registry. The study included 205 detected sex chromosome abnormality cases of which 93 (45%) were live births, 18 (9%) late fetal deaths, 37 (18%) early fetal deaths, and 57 (28%) elective terminations. Pregnancy outcome distribution varied by type of sex chromosome abnormality. Prenatal diagnosis was reported for 132 (64%) of the cases, of which 46 (35%) were subsequently electively terminated. Eleven cases were elective terminations where the sex chromosome abnormality was diagnosed after delivery. Elective termination rates subsequent to prenatal diagnosis differed by sex chromosome abnormality, being highest for 45,X (54%), followed by 47,XXY (46%), 47,XYY (29%), and 47,XXX (17%). Although prenatal diagnosis rates increased significantly over the time period (P = 0.006), the subsequent elective termination rate declined slightly, albeit the trend was not statistically significant (P = 0.440). The prenatal diagnosis rate was highest for the 35-39-year maternal age group, although this age group did not have subsequent elective termination rates higher than other maternal age groups. Pregnancy outcome distribution and prenatal diagnosis and subsequent elective termination of sex chromosome abnormalities appeared to depend on the type of sex chromosome abnormality, year of delivery, and maternal age.
诸如特纳综合征、克兰费尔特综合征、XXX综合征和47,XYY等性染色体异常可在产前诊断并选择性终止妊娠。本研究调查了1986年至1999年期间夏威夷产前和产后诊断出的性染色体异常的妊娠结局模式,并计算了各种因素的产前诊断率和随后的选择性终止妊娠率。数据来自全州基于人群的出生缺陷登记处。该研究包括205例检测到的性染色体异常病例,其中93例(45%)为活产,18例(9%)为晚期胎儿死亡,37例(18%)为早期胎儿死亡,57例(28%)为选择性终止妊娠。妊娠结局分布因性染色体异常类型而异。132例(64%)病例报告了产前诊断,其中46例(35%)随后被选择性终止妊娠。11例为分娩后诊断出性染色体异常的选择性终止妊娠病例。产前诊断后的选择性终止妊娠率因性染色体异常而异,45,X最高(54%),其次是47,XXY(46%)、47,XYY(29%)和47,XXX(17%)。尽管在此期间产前诊断率显著增加(P = 0.006),但随后的选择性终止妊娠率略有下降,尽管该趋势无统计学意义(P = 0.440)。35 - 39岁产妇年龄组的产前诊断率最高,尽管该年龄组随后的选择性终止妊娠率并不高于其他产妇年龄组。性染色体异常的妊娠结局分布、产前诊断以及随后的选择性终止妊娠似乎取决于性染色体异常类型、分娩年份和产妇年龄。