Glueck Charles J, Goldenberg Naila, Wang Ping, Aregawi Dawit
Cholesterol Center, Jewish Hospital, Cincinnati, Ohio, USA.
Clin Appl Thromb Hemost. 2004 Oct;10(4):365-71. doi: 10.1177/107602960401000409.
A kindred was examined in which the 48-year-old white female proband with three deep venous thrombosis-pulmonary emboli events had four thrombophilic and one hypofibrinolytic mutations, and in which her 14-year-old asymptomatic daughter had four thrombophilic mutations. The proband was heterozygous for the G1691A factor V Leiden, G20210A prothrombin, and platelet glycoprotein IIIa PL A1/A2 mutations, had high factor VIII (221%), and was homozygous for the 4G4G plasminogen activator inhibitor-1 gene mutation, with high plasminogen activator inhibitor activity (23.7 U/mL). Her 14-year-old daughter was homozygous for the G1691A factor V Leiden and platelet glycoprotein IIb-IIIa PL A2/A2 mutations, compound heterozygous for the C677T and A1298C methylenetetrahydrofolate reductase (MTHFR) mutations, and heterozygous for the G20210A prothrombin mutation, a combination with an estimated likelihood of 1.6 x 10(-7). In 247 white healthy controls, there was no V Leiden homozygosity and no V Leiden-prothrombin gene compound heterozygosity. Heterozygosity for the V Leiden and prothrombin gene mutations was 3.2% and 4.1%, respectively. Homozygosity for the platelet glycoprotein IIb-IIIa PL A2A2, PAI-1 gene 4G4G, and C677T MTHFR mutations was 3.2%, 22.7%, and 12%, respectively. The proband will receive anticoagulation therapy for life. Beyond aspirin, avoidance of exogenous estrogens, and enoxaparin prophylaxis during pregnancy, it is not known whether the proband's daughter should have lifelong anticoagulation therapy, or only after her first thrombotic event.
对一个家族进行了检查,其中48岁的白人女性先证者发生了3次深静脉血栓形成-肺栓塞事件,有4种血栓形成倾向和1种低纤维蛋白溶解突变,而她14岁无症状的女儿有4种血栓形成倾向突变。先证者为G1691A因子V莱顿、G20210A凝血酶原和血小板糖蛋白IIIa PLA1/A2突变的杂合子,因子VIII水平高(221%),并且是4G4G纤溶酶原激活物抑制剂-1基因突变的纯合子,纤溶酶原激活物抑制剂活性高(23.7 U/mL)。她14岁的女儿为G1691A因子V莱顿和血小板糖蛋白IIb-IIIa PLA2/A2突变的纯合子,C677T和A1298C亚甲基四氢叶酸还原酶(MTHFR)突变的复合杂合子,以及G20210A凝血酶原突变的杂合子,这种组合估计可能性为1.6×10(-7)。在247名白人健康对照中,没有因子V莱顿纯合子,也没有因子V莱顿-凝血酶原基因复合杂合子。因子V莱顿和凝血酶原基因突变的杂合子分别为3.2%和4.1%。血小板糖蛋白IIb-IIIa PLA2A2、PAI-1基因4G4G和C677T MTHFR突变的纯合子分别为3.2%、22.7%和12%。先证者将接受终身抗凝治疗。除了服用阿司匹林、避免外源性雌激素以及孕期使用依诺肝素进行预防外,尚不清楚先证者的女儿是否应接受终身抗凝治疗,还是仅在她首次发生血栓事件后才进行治疗。