Puzianowska-Kuznicka Monika, Kuznicki Jacek
Department of Endocrinology, Medical Research Center, Polish Academy of Sciences, 1a Banacha Street, 02-097 Warsaw, Poland.
Int J Biochem Cell Biol. 2005 May;37(5):947-60. doi: 10.1016/j.biocel.2004.10.011. Epub 2004 Dec 15.
The molecular mechanisms leading to human senescence are still not known mostly because of the complexity of the process. Different research approaches are used to study ageing including studies of monogenic segmental progeroid syndromes. None of the known progerias represents true precocious ageing. Some of them, including Werner (WS), Bloom (BS), and Rothmund-Thomson syndromes (RTS) as well as combined xeroderma pigmentosa-Cockayne syndrome (XP-CS) are characterised by features resembling precocious ageing and the increased risk of malignant disease. Such phenotypes result from the mutations of the genes encoding proteins involved in the maintenance of genomic integrity, in most cases DNA helicases. Defective functioning of these proteins affects DNA repair, recombination, replication and transcription. Other segmental progeroid syndromes, such as Hutchinson-Gilford progeria (HGPS) and Cockayne syndrome are not associated with an increased risk of cancer. In this paper we present the clinical and molecular features of selected progeroid syndromes and describe the potential implications of these data for studies of ageing and cancer development.
导致人类衰老的分子机制大多仍不为人所知,主要是因为这个过程十分复杂。人们运用了不同的研究方法来研究衰老,包括对单基因节段性早衰综合征的研究。已知的早衰症中没有一种代表真正的早衰。其中一些,包括沃纳综合征(WS)、布卢姆综合征(BS)、罗特蒙德-汤姆森综合征(RTS)以及色素性干皮病-科凯恩综合征(XP-CS),其特征是具有类似早衰的特点以及患恶性疾病的风险增加。这些表型是由编码参与维持基因组完整性的蛋白质的基因突变引起的,在大多数情况下是DNA解旋酶。这些蛋白质的功能缺陷会影响DNA修复、重组、复制和转录。其他节段性早衰综合征,如哈钦森-吉尔福德早衰症(HGPS)和科凯恩综合征,与癌症风险增加无关。在本文中,我们介绍了所选早衰综合征的临床和分子特征,并描述了这些数据对衰老和癌症发展研究的潜在意义。