Yang Ming-Shiang, Chen Clayton Chi-Chang, Cheng Yung-Yi, Tyan Yeu-Sheng, Wang Yi-Fen, Lee San-Kan
Department of Radiology, Chung-Shan Medical University Hospital, Taichung, Taiwan.
J Formos Med Assoc. 2005 Feb;104(2):129-32.
Wolfram syndrome is a rare diffuse neurodegenerative disorder also known as DIDMOAD due to its characteristics of diabetes insipidus, diabetes mellitus, optic nerve atrophy and deafness. It is also associated with a wide variety of abnormalities of the central nervous system, urinary tract and endocrine glands. It may be familial or sporadic. Imaging findings include absence of the short T1 nature of the pituitary posterior lobe, atrophy of the optic nerve, chiasma, and tracts. Atrophy of the brain stem and cerebellum has also been reported. We describe a 15-year-old boy and an 11-year-old girl with Wolfram syndrome who were siblings from a diabetes mellitus family. They received regular insulin control at our hospital and had symptoms of frequent urinary tract infection and diabetes insipidus. Magnetic resonance imaging revealed marked pons and cerebellar atrophy. Optic nerve and chiasma atrophy was also noted.
沃夫勒姆综合征是一种罕见的弥漫性神经退行性疾病,因其具有尿崩症、糖尿病、视神经萎缩和耳聋的特征,也被称为DIDMOAD。它还与中枢神经系统、泌尿系统和内分泌腺的多种异常有关。它可能是家族性的或散发性的。影像学表现包括垂体后叶短T1信号消失、视神经、视交叉和视束萎缩。也有脑干和小脑萎缩的报道。我们描述了一名15岁男孩和一名11岁女孩,他们患有沃夫勒姆综合征,是来自一个糖尿病家族的兄弟姐妹。他们在我们医院接受常规胰岛素治疗,有频繁尿路感染和尿崩症的症状。磁共振成像显示脑桥和小脑明显萎缩。还发现了视神经和视交叉萎缩。