Hazan Carole, Orlow Seth J, Schaffer Julie V
Department of Dermatology, New York University School of Medicine, USA.
Dermatol Online J. 2005 Dec 30;11(4):12.
A 13-year-old boy presented with a lifelong history of tightly-adherent, brown, polygonal scales that covered the extensor surfaces of the extremities, lateral aspects of the trunk, and neck. The clinical presentation and the history of a similar skin condition in the patient's male maternal relatives helped establish the diagnosis of X-linked recessive ichthyosis (XLI). Systemic manifestations of the steroid sulfatase (STS) deficiency underlying XLI include cryptorchidism, asymptomatic corneal opacities, and maternal failure to progress during labor. Most cases of XLI are caused by deletions of the STS gene, and contiguous gene syndromes may occur when the deletions extend to neighboring genes on the distal short arm of the X chromosome.
一名13岁男孩,有终生的皮肤病史,其四肢伸侧、躯干侧面和颈部覆盖着紧密附着的褐色多边形鳞屑。患者男性母系亲属有类似皮肤病史,结合临床表现,有助于诊断X连锁隐性鱼鳞病(XLI)。XLI潜在的类固醇硫酸酯酶(STS)缺乏的全身表现包括隐睾、无症状角膜混浊以及母亲分娩时产程停滞。大多数XLI病例是由STS基因缺失引起的,当缺失延伸到X染色体短臂远端的相邻基因时,可能会出现连续基因综合征。