Collinge J, Poulter M, Davis M B, Baraitser M, Owen F, Crow T J, Harding A E
Division of Psychiatry, Clinical Research Centre, Harrow, England.
Am J Hum Genet. 1991 Dec;49(6):1351-4.
The identification of defects in the prion protein (PrP) gene in families with inherited Creutzfeldt-Jakob disease or Gerstmann-Straussler syndrome allows presymptomatic diagnosis or exclusion of these disorders in subjects at risk. After counseling, PrP gene analysis was performed in three such individuals: two from families with a 144-bp insert and one with a point mutation at codon 102 in the PrP gene. The presence of a PrP gene defect was confirmed in one and excluded in two. Despite the potential problems of using PrP gene analysis in genetic prediction - specifically, uncertainty about penetrance and, generally, problems of presymptomatic testing in any inherited late-onset neurodegenerative disorder - we conclude that it has a role to play in improved genetic counseling for families with inherited prion diseases.
在患有遗传性克雅氏病或格斯特曼-施特劳斯勒综合征的家族中,对朊病毒蛋白(PrP)基因缺陷的鉴定使得能够对有风险的个体进行症状前诊断或排除这些疾病。在进行咨询后,对三名此类个体进行了PrP基因分析:两名来自有144碱基对插入片段的家族,一名在PrP基因的第102密码子处有一个点突变。其中一名个体被证实存在PrP基因缺陷,两名个体被排除。尽管在遗传预测中使用PrP基因分析存在潜在问题——特别是外显率的不确定性,以及一般来说在任何遗传性迟发性神经退行性疾病中进行症状前检测的问题——但我们得出结论,它在改善遗传性朊病毒疾病家族的遗传咨询方面具有作用。