Ribeiro Maria do Céu, Gama de Sousa Susana, Freitas Manuela Mota, Carrilho Inês, Fernandes Isilda
Pediatrics Department, S João Hospital, Porto, Portugal.
Pediatr Neurol. 2007 Jun;36(6):418-20. doi: 10.1016/j.pediatrneurol.2007.01.015.
Polymalformative syndromes are always a clinical challenge for their complexity and sometimes for their rarity. Authors present the case of a girl with peculiar facies, macrocephaly, axial hypotonia, and severe development delay. Cerebral magnetic resonance showed polymicrogyria. Cytogenetics revealed a 46,XX,der(1)(qter-->p36.13::q42.3-->qter) karyotype. This is the third case described to date. Isolated partial deletions or trisomy, although rare, are more frequently reported. None of these genetic findings has ever been related with polymicrogyria. Molecular cytogenetic characterization was in this case of great value.
多畸形综合征因其复杂性以及有时因其罕见性,始终是一项临床挑战。作者报告了一名具有特殊面容、巨头畸形、轴性肌张力减退和严重发育迟缓的女孩病例。脑部磁共振成像显示多小脑回。细胞遗传学检查显示核型为46,XX,der(1)(qter→p36.13::q42.3→qter)。这是迄今为止报道的第三例病例。孤立的部分缺失或三体虽然罕见,但报道更为频繁。这些基因发现均未曾与多小脑回相关联。在该病例中,分子细胞遗传学特征具有重要价值。