Ganapathi Karthik A, Shimamura Akiko
Department of Haematology/Oncology, Children's Hospital/Dana Farber Cancer Institute, Boston, MA, USA.
Br J Haematol. 2008 May;141(3):376-87. doi: 10.1111/j.1365-2141.2008.07095.x.
Impairment of ribosome biogenesis or function characterizes several of the inherited bone marrow failure syndromes: Diamond-Blackfan anaemia, dyskeratosis congenita (DC), Shwachman-Diamond syndrome and cartilage-hair hypoplasia. These syndromes exhibit overlapping but distinct clinical phenotypes and each disorder involves different aspects of ribosomal biogenesis. The clinical characteristics of each syndrome are briefly reviewed. Molecular studies of ribosome biogenesis and function in each of these syndromes are discussed. Models of how impairment of ribosomal pathways might affect haematopoiesis and tumorigenesis are explored.
钻石-黑范贫血、先天性角化不良(DC)、施-戴综合征和软骨毛发发育不全。这些综合征表现出重叠但不同的临床表型,每种疾病涉及核糖体生物合成的不同方面。本文简要回顾了每种综合征的临床特征。讨论了这些综合征中核糖体生物合成和功能的分子研究。探讨了核糖体途径受损可能影响造血和肿瘤发生的模型。