Yukawa Sonosuke, Tahara Koichiro, Shoji Aki, Hayashi Haeru, Tsuboi Norioki
Department of Rheumatology, Tokyo Medical University, 6-7-1 Nishishinjuku, Shinjuku-ku, Tokyo, 160-0023, Japan.
Mod Rheumatol. 2008;18(5):516-21. doi: 10.1007/s10165-008-0087-3. Epub 2008 Jun 13.
A 32-year-old woman was diagnosed with leucopenia in 2002, being antinuclear antibody, anti-DNA antibody, and antiphospholipid antibody positive, and she was administered low-dose aspirin. In July 2006, she was admitted to our hospital because of pyrexia and abdominal pain. Examination revealed paralytic ileus, absence of the pupillary light reflex, dyshidrosis and anuresis. In addition, with high-level interleukin-6 in cerebrospinal fluid, the sensory nerve conduction velocity was derivation impotence. She was subsequently diagnosed with systemic lupus erythematosus (SLE) with central nervous system involvement, peripheral neuropathy as well as acute pan-dysautonomia. After pulse corticosteroid therapy, paralytic ileus was improved, however, the urination disorder persisted, and syncope due to orthostatic hypotension became marked. Plasma exchange and a second course of pulse corticosteroid therapy were performed, and were ineffective, whereas intravenous cyclophosphamide was effective. This patient is a rare case of central nervous system, peripheral neuropathy as well as acute pan-dysautonomia with SLE.
一名32岁女性于2002年被诊断为白细胞减少症,抗核抗体、抗DNA抗体和抗磷脂抗体呈阳性,接受了小剂量阿司匹林治疗。2006年7月,她因发热和腹痛入住我院。检查发现麻痹性肠梗阻、瞳孔对光反射消失、出汗障碍和无尿。此外,脑脊液中白细胞介素-6水平升高,感觉神经传导速度推导无力。随后她被诊断为系统性红斑狼疮(SLE)伴中枢神经系统受累、周围神经病变以及急性全自主神经功能不全。经过脉冲皮质类固醇治疗后,麻痹性肠梗阻有所改善,但排尿障碍持续存在,直立性低血压导致的晕厥变得明显。进行了血浆置换和第二个疗程的脉冲皮质类固醇治疗,但均无效,而静脉注射环磷酰胺有效。该患者是SLE伴中枢神经系统、周围神经病变以及急性全自主神经功能不全的罕见病例。