Tarnowski Maciej, Sieroń Aleksander L
Katedry Biologii Ogólnej, Molekularnej i Genetyki Slaskiego Uniwersytetu Medycznego w Katowicach.
Wiad Lek. 2008;61(4-6):166-72.
A congenital brittle bone disease, also named osteogenesis imperfecta (OI) is a genetic bone dysplasia with wide spectrum of clinical manifestations, from almost normal, through mild to severe phenotypes or even lethal. The most severe type of OI, type II, is characterized by significant bone deformations, resulting from frequent bone fractures occurring already in utero as well as after birth, due to bone fragility causing fractures even during regular newborn handling. Children with this type of OI die during first few weeks after birth due to poor circulatory/pulmonary conditions resulting from ribs and vertebral deformations. Currently, there is a lack of successful treatment and the therapy is restricted to applications of orthopedic equipment or administration of bisfosfonian, but both with limited success. The therapy of the future is cell therapy where the mesenchymal cells following transplantation undergo differentiation to bone marrow cells and take over the function of new and correct bone formation. In his review, both the current achievements as well as future perspectives are discussed.
一种先天性脆性骨病,也称为成骨不全症(OI),是一种具有广泛临床表现的遗传性骨发育不良,从几乎正常到轻度至重度表型,甚至是致命的。OI最严重的类型,即II型,其特征是明显的骨骼变形,这是由于在子宫内以及出生后频繁发生骨折所致,由于骨骼脆弱,即使在常规的新生儿护理过程中也会导致骨折。患有这种类型OI的儿童在出生后的头几周内由于肋骨和脊柱变形导致的循环/肺部状况不佳而死亡。目前,缺乏成功的治疗方法,治疗仅限于使用矫形设备或给予双膦酸盐,但两者的成功率都有限。未来的治疗方法是细胞治疗,间充质细胞在移植后会分化为骨髓细胞,并承担新的和正确的骨形成功能。在他的综述中,讨论了当前的成就以及未来的前景。