Forshew Tim, Tatevossian Ruth G, Lawson Andrew R J, Ma Jing, Neale Geoff, Ogunkolade Babatunji W, Jones Tania A, Aarum Johan, Dalton James, Bailey Simon, Chaplin Tracy, Carter Rowena L, Gajjar Amar, Broniscer Alberto, Young Bryan D, Ellison David W, Sheer Denise
Neuroscience Centre, Barts and The London School of Medicine and Dentistry, Queen Mary University of London, Institute of Cell and Molecular Science, London, UK.
J Pathol. 2009 Jun;218(2):172-81. doi: 10.1002/path.2558.
We report genetic aberrations that activate the ERK/MAP kinase pathway in 100% of posterior fossa pilocytic astrocytomas, with a high frequency of gene fusions between KIAA1549 and BRAF among these tumours. These fusions were identified from analysis of focal copy number gains at 7q34, detected using Affymetrix 250K and 6.0 SNP arrays. PCR and sequencing confirmed the presence of five KIAA1549-BRAF fusion variants, along with a single fusion between SRGAP3 and RAF1. The resulting fusion genes lack the auto-inhibitory domains of BRAF and RAF1, which are replaced in-frame by the beginning of KIAA1549 and SRGAP3, respectively, conferring constitutive kinase activity. An activating mutation of KRAS was identified in the single pilocytic astrocytoma without a BRAF or RAF1 fusion. Further fusions and activating mutations in BRAF were identified in 28% of grade II astrocytomas, highlighting the importance of the ERK/MAP kinase pathway in the development of paediatric low-grade gliomas.
我们报告了在100%的后颅窝毛细胞型星形细胞瘤中激活ERK/MAP激酶通路的基因畸变,在这些肿瘤中KIAA1549与BRAF之间基因融合的频率很高。这些融合是通过对7q34处的局灶性拷贝数增加进行分析鉴定出来的,使用Affymetrix 250K和6.0 SNP阵列进行检测。PCR和测序证实存在5种KIAA1549 - BRAF融合变体,以及1种SRGAP3与RAF1之间的融合。产生的融合基因缺乏BRAF和RAF1的自抑制结构域,分别被KIAA1549和SRGAP3的起始部分框内取代,赋予了组成型激酶活性。在单个无BRAF或RAF1融合的毛细胞型星形细胞瘤中鉴定出KRAS的激活突变。在28%的II级星形细胞瘤中还鉴定出BRAF的进一步融合和激活突变,突出了ERK/MAP激酶通路在儿童低级别胶质瘤发生中的重要性。