Sawanobori E, Umino A, Kanai H, Matsushita K, Iwasa S, Kitamura H, Oda T, Yoshizawa N, Sugita K, Higashida K
1Department of Pediatrics, Interdisciplinary Graduate School of Medicine and Engineering, University of Yamanashi, Japan.
Clin Nephrol. 2009 Jun;71(6):703-7. doi: 10.5414/cnp71703.
We herein report the case of a 12-year-old boy with dense deposit disease (DDD) evoked by streptococcal infection. He had been diagnosed to have asymptomatic hematuria syndrome at the age of 6 during school screening. At 12 years of age, he was found to have macrohematuria and overt proteinuria with hypocomplementemia 2 months after streptococcal pharyngitis. Renal biopsy showed endocapillary proliferative glomerulonephritis with double contours of the glomerular basement membrane. Hypocomplementemia and proteinuria were sustained for over 8 weeks. He was suspected to have dense deposit disease due to intramembranous deposits in the first and the second biopsies. 1 month after treatment with methylprednisolone pulse therapy, proteinuria decreased to a normal level. Microscopic hematuria disappeared 2 years later, but mild hypocomplementemia persisted for more than 7 years. Nephritis-associated plasmin receptor (NAPlr), a nephritic antigen for acute poststreptococcal glomerulonephritis, was found to be positive in the glomeruli for more than 8 weeks. DDD is suggested to be caused by dysgeneration of the alternative pathway due to C3NeF and impaired Factor H activity. A persistent deposition of NAPlr might be one of the factors which lead to complement dysgeneration. A close relationship was suggested to exist between the streptococcal infection and dense deposit disease in this case.
我们在此报告一例由链球菌感染引发致密物沉积病(DDD)的12岁男孩病例。他在6岁时学校筛查中被诊断为无症状血尿综合征。12岁时,他在链球菌性咽炎2个月后出现肉眼血尿、明显蛋白尿及低补体血症。肾活检显示毛细血管内增生性肾小球肾炎伴肾小球基底膜双轨征。低补体血症和蛋白尿持续超过8周。由于首次及第二次活检中存在膜内沉积物,怀疑他患有致密物沉积病。甲基强的松龙冲击治疗1个月后,蛋白尿降至正常水平。镜下血尿2年后消失,但轻度低补体血症持续超过7年。肾炎相关纤溶酶受体(NAPlr),一种急性链球菌感染后肾小球肾炎的肾炎抗原,在肾小球中呈阳性超过8周。致密物沉积病被认为是由于C3NeF导致替代途径异常激活及因子H活性受损所致。NAPlr的持续沉积可能是导致补体异常激活的因素之一。该病例提示链球菌感染与致密物沉积病之间存在密切关系。