Department of Dermatology, University of Lübeck, 23538 Lübeck, Germany.
Clin Exp Dermatol. 2010 Aug;35(6):614-7. doi: 10.1111/j.1365-2230.2009.03731.x. Epub 2009 Oct 23.
Anti-p200 pemphigoid and bullous pemphigoid (BP) are autoimmune subepidermal blistering diseases characterized by autoantibodies to a 200-kDa dermal antigen (p200) and two hemidesmosomal proteins (BP180 and BP230), respectively. We report a 70-year-old man with haemorrhagic blisters, widespread crusted erosions, and the immunopathological characteristics of anti-p200 pemphigoid. Treatment with doxycycline, topical corticosteroids and immunoadsorption led to rapid clinical remission. However, 19 weeks later, a relapse occurred with generalized itchy urticarial erythema and tense blisters. At this time, both strong dermal and epidermal IgG staining was detected by indirect immunofluorescence microscopy on salt-split skin, and autoantibodies against both p200 and the 16th noncollagenous (NC16A) domain of BP180 were found. Interestingly, the relapse was associated not only with the detection of autoantibodies to a second autoantigen (BP180), but also with an altered clinical phenotype. This case was a unique occasion to directly monitor the emergence of intermolecular epitope spreading during the course of an autoimmune bullous disorder.
抗 p200 天疱疮和大疱性类天疱疮 (BP) 是两种自身免疫性表皮下水疱性疾病,其特征分别为针对 200kDa 真皮抗原 (p200) 和两种半桥粒蛋白 (BP180 和 BP230) 的自身抗体。我们报告了一例 70 岁男性,表现为出血性水疱、广泛结痂糜烂,且具有抗 p200 天疱疮的免疫病理学特征。多西环素、局部皮质类固醇和免疫吸附治疗导致快速临床缓解。然而,19 周后,出现全身性瘙痒性荨麻疹性红斑和紧张性水疱的复发。此时,盐裂皮肤间接免疫荧光显微镜检查显示强烈的真皮和表皮 IgG 染色,并且检测到针对 p200 和 BP180 的第 16 个非胶原 (NC16A) 结构域的自身抗体。有趣的是,复发不仅与针对第二种自身抗原 (BP180) 的自身抗体的检测有关,而且与改变的临床表型有关。该病例是在自身免疫性大疱性疾病过程中直接监测到分子间表位扩展出现的独特情况。