James Homer Wright Pathology Laboratories, Massachusetts General Hospital, Boston, 02114, USA.
Am J Surg Pathol. 2011 Nov;35(11):1666-78. doi: 10.1097/PAS.0b013e31822832de.
Nodular lymphocyte-predominant Hodgkin lymphoma (NLPHL) is a distinct Hodgkin lymphoma subtype composed of few neoplastic lymphocyte-predominant (LP) cells in a background of reactive small B and T cells. We have seen occasional NLPHL cases that contain background T cells with prominent cytologic atypia, raising the differential diagnosis of peripheral T-cell lymphoma not otherwise specified (PTCL-NOS) or a composite lymphoma. We sought to characterize the clinicopathologic features of such cases. Eleven NLPHL cases with atypical T cells diagnosed from 1977 to 2010 were identified at 2 institutions and compared with 24 control NLPHL cases lacking atypical T cells. All 9 male patients and 2 female patients presented with localized peripheral lymphadenopathy. In comparison with control patients, they were younger (median age, 13.8 vs. 36.1 y; P=0.015), with more frequent cervical lymph node involvement (54.5% vs. 8.3%, P=0.015). In all 11 cases, areas of NLPHL with typical B-cell-rich nodules containing LP cells were present. Nine cases contained sheets of atypical T cells surrounding primary and secondary follicles in a pattern mimicking the T-zone pattern of PTCL-NOS; the remaining 2 cases contained atypical T cells presented as large clusters at the periphery of B-cell-rich nodules. In all cases, the atypical T-cell-rich areas contained rare scattered LP cells, which were IgD in 5 of 7 cases (71.4%). The atypical T cells showed no pan-T-cell antigen loss or aberrant T-cell antigen expression in any case, and polymerase chain reaction or Southern blot analysis showed no evidence of T-cell clonality in 6 cases tested. The atypical T cells exhibited a variable immunophenotype with respect to germinal center, follicular T-helper, T-regulatory, and cytotoxic T-cell markers. Among 8 patients with clinical follow-up (median follow-up: 6.4 y), 5 patients had recurrent NLPHL at 6 months to 12 years after diagnosis and 6 patients are alive without disease at 9 months to 18 years after diagnosis. In comparison with control patients, NLPHL patients with atypical T cells were more likely to develop recurrent NLPHL (71.4% vs. 13.6%, P=0.008) and to have a shorter time to relapse (P=0.04). Our findings suggest that some cases of NLPHL, occurring predominantly in younger patients, contain prominent populations of morphologically atypical T cells that may raise the possibility of concurrent nodal involvement by PTCL-NOS, a rare diagnosis in children. The clinical behavior of these cases appears similar to that of NLPHL with T-cell-rich diffuse areas, with a higher risk of disease recurrence and no difference in overall survival; however, this finding warrants confirmation in studies of larger numbers of patients.
结节性淋巴细胞为主型霍奇金淋巴瘤(NLPHL)是一种独特的霍奇金淋巴瘤亚型,由反应性小 B 和 T 细胞背景中的少数肿瘤性淋巴细胞为主(LP)细胞组成。我们偶尔会遇到包含具有明显细胞学异型性的背景 T 细胞的 NLPHL 病例,这增加了外周 T 细胞淋巴瘤非特指型(PTCL-NOS)或复合淋巴瘤的鉴别诊断。我们试图描述这些病例的临床病理特征。在 2 家机构中,从 1977 年至 2010 年诊断出 11 例伴有异型 T 细胞的 NLPHL 病例,并与 24 例缺乏异型 T 细胞的对照 NLPHL 病例进行比较。所有 9 例男性患者和 2 例女性患者均表现为局部外周淋巴结病。与对照患者相比,他们更年轻(中位年龄,13.8 岁 vs. 36.1 岁;P=0.015),更常发生颈部淋巴结受累(54.5% vs. 8.3%;P=0.015)。在所有 11 例患者中,均存在含有 LP 细胞的典型富含 B 细胞结节的 NLPHL 区。9 例病例含有围绕原发性和次级滤泡的异型 T 细胞片层,模式类似于 PTCL-NOS 的 T 区模式;其余 2 例病例含有异型 T 细胞,以大簇形式位于富含 B 细胞结节的外周。在所有病例中,异型 T 细胞丰富区均含有罕见的散在 LP 细胞,其中 71.4%(5/7)为 IgD。在任何病例中,异型 T 细胞均未表现出全 T 细胞抗原缺失或异常 T 细胞抗原表达,在 6 例检测的病例中,聚合酶链反应或 Southern 印迹分析均未显示 T 细胞克隆性。异型 T 细胞表现出与生发中心、滤泡 T 辅助细胞、T 调节细胞和细胞毒性 T 细胞标志物有关的可变免疫表型。在 8 例具有临床随访的患者(中位随访:6.4 年)中,5 例患者在诊断后 6 个月至 12 年内复发 NLPHL,6 例患者在诊断后 9 个月至 18 年内无疾病存活。与对照患者相比,伴有异型 T 细胞的 NLPHL 患者更有可能出现复发 NLPHL(71.4% vs. 13.6%;P=0.008),且复发时间更短(P=0.04)。我们的研究结果表明,一些 NLPHL 病例主要发生在年轻患者中,含有明显形态异型性的 T 细胞群体,这可能增加了同时存在罕见儿童诊断的 PTCL-NOS 淋巴结受累的可能性。这些病例的临床行为与富含 T 细胞的弥漫性区域的 NLPHL 相似,疾病复发风险较高,但总生存无差异;然而,这一发现需要在更大数量患者的研究中得到证实。