Moores UCSD Cancer Center, University of California, San Diego, La Jolla, CA 92093, USA.
Blood. 2012 Mar 29;119(13):3155-63. doi: 10.1182/blood-2011-04-350694. Epub 2012 Jan 5.
The t(8;21)(q22;q22) is common in adult acute myeloid leukemia (AML). The RUNX1-ETO fusion protein that is expressed by this translocation is poorly leukemogenic and requires additional mutations for transformation. Loss of sex chromosome (LOS) is frequently observed in t(8;21) AML. In the present study, to evaluate whether LOS cooperates with t(8;21) in leukemogenesis, we first used a retroviral transduction/transplantation model to express RUNX1-ETO in hematopoietic cells from XO mice. The low frequency of leukemia in these mice suggests that the potentially critical gene for suppression of t(8;21) leukemia in humans is not conserved on mouse sex chromosomes. The gene encoding the GM-CSF receptor α subunit (CSF2RA) is located on X and Y chromosomes in humans but on chromosome 19 in mice. GM-CSF promotes myeloid cell survival, proliferation, and differentiation. To determine whether GM-CSF signaling affects RUNX1-ETO leukemogenesis, hematopoietic stem/progenitor cells that lack GM-CSF signaling were used to express RUNX1-ETO and transplanted into lethally irradiated mice, and a high penetrance of AML was observed in recipients. Furthermore, GM-CSF reduced the replating ability of RUNX1-ETO-expressing cells. These results suggest a possible tumor-suppressor role of GM-CSF in RUNX1-ETO leukemia. Loss of the CSF2RA gene may be a critical mutation explaining the high incidence of LOS associated with the t(8;21)(q22;q22) translocation.
t(8;21)(q22;q22) 在成人急性髓系白血病 (AML) 中较为常见。该易位表达的 RUNX1-ETO 融合蛋白的致白血病能力较弱,并且需要额外的突变才能转化。性染色体丢失 (LOS) 在 t(8;21)AML 中经常观察到。在本研究中,为了评估 LOS 是否与 t(8;21)在白血病发生中合作,我们首先使用逆转录病毒转导/移植模型在 XO 小鼠的造血细胞中表达 RUNX1-ETO。这些小鼠中白血病的低发生率表明,在人类中抑制 t(8;21)白血病的潜在关键基因在小鼠性染色体上并不保守。编码 GM-CSF 受体 α 亚基 (CSF2RA) 的基因在人类的 X 和 Y 染色体上,但在小鼠的 19 号染色体上。GM-CSF 促进髓系细胞的存活、增殖和分化。为了确定 GM-CSF 信号是否影响 RUNX1-ETO 白血病的发生,我们使用缺乏 GM-CSF 信号的造血干/祖细胞来表达 RUNX1-ETO,并将其移植到致死性照射的小鼠中,结果观察到受体中 AML 的高穿透率。此外,GM-CSF 降低了表达 RUNX1-ETO 的细胞的再平板能力。这些结果表明 GM-CSF 在 RUNX1-ETO 白血病中可能具有肿瘤抑制作用。CSF2RA 基因的缺失可能是解释与 t(8;21)(q22;q22)易位相关的 LOS 高发生率的关键突变。