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与精神性烦渴相关的急性前间隔综合征

Acute anterior compartment syndrome associated with psychogenic polydipsia.

作者信息

Maiocchi Licia, Bernardi Elsa

机构信息

Macquarie Hospital, North Ryde, NSW, Australia.

出版信息

Australas Psychiatry. 2012 Apr;20(2):159-61. doi: 10.1177/1039856211432465. Epub 2012 Mar 26.

DOI:10.1177/1039856211432465
PMID:22452903
Abstract

OBJECTIVE

The aim of this paper is to describe the association of psychogenic polydipsia with anterior compartment syndrome.

METHOD

Case report.

RESULTS

A 31-year-old man with glucose-6-phosphate-dehydrogenase (G6PD) deficiency had a history of paranoid schizophrenia from age 16 complicated by the use of drugs. Four years after the initial diagnosis of schizophrenia, he developed psychogenic polydipsia. This was complicated by episodic severe acute hyponatraemia with seizures and, on one occasion, by generalized rhabdomyolysis. One episode of severe acute hyponatraemia with delirium led to anterior compartment syndrome in both legs. Delayed diagnosis and treatment led to extensive myonecrosis and permanent bilateral foot drop. For 6 years his polydipsia remained partially controlled in a locked psychiatric ward with limited leave, until his sudden death related to severe water intoxication.

CONCLUSIONS

Anterior compartment syndrome is a rare event associated with psychogenic polydipsia. Psychiatrists, physicians and surgeons should be aware of the seriousness of anterior compartment syndrome and its potential to increase morbidity in patients with psychogenic polydipsia.

摘要

目的

本文旨在描述精神性烦渴与骨筋膜室综合征的关联。

方法

病例报告。

结果

一名31岁葡萄糖-6-磷酸脱氢酶(G6PD)缺乏症男性,自16岁起患有偏执型精神分裂症,并有药物使用史。精神分裂症初诊四年后,他出现了精神性烦渴。这并发了伴有癫痫发作的间歇性严重急性低钠血症,有一次还并发了全身性横纹肌溶解。一次伴有谵妄的严重急性低钠血症发作导致双腿出现骨筋膜室综合征。诊断和治疗延误导致广泛的肌肉坏死和永久性双侧足下垂。六年来,他的烦渴在一个封闭的精神科病房中得到部分控制,外出受限,直到他因严重水中毒突然死亡。

结论

骨筋膜室综合征是与精神性烦渴相关的罕见事件。精神科医生、内科医生和外科医生应意识到骨筋膜室综合征的严重性及其增加精神性烦渴患者发病率的可能性。

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Rare times rare: The hyponatremia, rhabdomyolysis, anterior compartment syndrome sequence.罕见情况之罕见:低钠血症、横纹肌溶解症、前间隔综合征序列。
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