Cui Qin, Wang Wen, Fu Zhenzhen, Shao Xin, Zhang Zhihong, Zhang Mei, Ju Xianxia, Wang Kunlin, Chen Jiawei, Zhou Hongwen
Department of Geriatrics, Department of Cadres, Tong Ling People's Hospital, Tongling, Anhui 244000, China;
J Biomed Res. 2013 Mar;27(2):145-50. doi: 10.7555/JBR.27.20120121. Epub 2013 Feb 20.
Multiple endocrine neoplasia type 2A (MEN2A), a subtype of MEN2, is characterized by medullary thyroid cancer, pheochromocytoma, and primary hyperparathyroidism. A Han Chinese pedigree with MEN2A was investigated following confirmation of the proband's diagnosis by pathological findings and DNA/biochemical screening. DNA samples from 4 other family members were collected and exon 5, 8, 10, 11, 13, 16 and 18 of the RET proto-oncogene were sequenced and then analyzed. A missense mutation of TGG (Trp) to TGC (Cys) at codon 634 (the classic MEN2A mutation) in exon 11 of the RET gene was detected in 3 family members, including the proband. Sequencing data were compared with the human gene mutation database. Elevated serum calcitonin level was detected initially; medullary thyroid carcinoma was revealed in the 3 cases and adrenal pheochromocytoma was also found in the proband. Elective operations were successfully performed on the adrenal and thyroid glands because of pheochromocytoma and medullary thyroid carcinoma. Our case study confirms that integrated DNA-based/biochemical screening is crucial for early diagnosis of MEN2A and is helpful in the screening of their relatives. In addition, DNA-based screening may occasionally uncover a previously unknown RET sequence.
2A型多发性内分泌腺瘤病(MEN2A)是MEN2的一种亚型,其特征为甲状腺髓样癌、嗜铬细胞瘤和原发性甲状旁腺功能亢进。在通过病理检查结果以及DNA/生化筛查确诊先证者的诊断后,对一个患有MEN2A的汉族家系进行了调查。收集了其他4名家庭成员的DNA样本,对RET原癌基因的第5、8、10、11、13、16和18外显子进行测序,然后进行分析。在包括先证者在内的3名家庭成员中,检测到RET基因第11外显子第634密码子处存在由TGG(色氨酸)突变为TGC(半胱氨酸)的错义突变(经典的MEN2A突变)。将测序数据与人类基因突变数据库进行了比较。最初检测到血清降钙素水平升高;3例患者均被诊断为甲状腺髓样癌,先证者还被发现患有肾上腺嗜铬细胞瘤。由于嗜铬细胞瘤和甲状腺髓样癌,成功地对肾上腺和甲状腺进行了择期手术。我们的病例研究证实,基于DNA的综合/生化筛查对于MEN2A的早期诊断至关重要,有助于对其亲属进行筛查。此外,基于DNA的筛查偶尔可能会发现以前未知的RET序列。