Serikawa Takehiro, Nishiyama Kenichi, Tohyama Jun, Tazawa Ryushi, Goto Kiyoe, Kuriyama Yoko, Haino Kazufumi, Kanemura Yonehiro, Yamasaki Mami, Nakata Koh, Takakuwa Koichi, Enomoto Takayuki
Department of Obstetrics and Gynecology, Niigata University Medical and Dental Hospital, Niigata, Japan.
Congenit Anom (Kyoto). 2014 Nov;54(4):243-5. doi: 10.1111/cga.12069.
We present a case of a patient whose L1CAM gene in X-chromosome has a C924T transition. Her first son's ventriculomegaly was prenatally detected. A mature infant was born, his head circumference was large, and thumbs were bilaterally adducted. X-linked hydrocephalus (XLH) was suspected. The DNA examination revealed that both her and boy's LICAM gene had a C924T transition. She became pregnant 5 years later and amniocentesis was performed. The results of cytogenetic analysis revealed that the fetus was female. She continued her pregnancy and delivered a healthy girl. She again became pregnant 3 years later. The chromosomal analysis revealed that the fetus was male. Fetal DNA analysis determined that the fetus had the inherited mutation. She chose to terminate the pregnancy. A C924T mutation can be disease causing for XLH, and the detection of this mutation would aid in genetic counseling for the prenatal diagnosis of XLH.
我们报告一例患者,其X染色体上的L1CAM基因发生了C924T转换。她的第一个儿子在产前被检测出脑室扩大。出生时是一个成熟婴儿,头围较大,双侧拇指内收。怀疑为X连锁脑积水(XLH)。DNA检查显示她和男孩的LICAM基因均有C924T转换。5年后她再次怀孕并进行了羊水穿刺。细胞遗传学分析结果显示胎儿为女性。她继续妊娠并生下一个健康女孩。3年后她又怀孕了。染色体分析显示胎儿为男性。胎儿DNA分析确定胎儿具有遗传性突变。她选择终止妊娠。C924T突变可能导致XLH,该突变的检测将有助于XLH产前诊断的遗传咨询。