Zhao Rui-jiao, Wu Kai-yan, Zhang Jian-guo, Ma Yi-hui, Kong Ling-fei
Department of Pathology, The People's Hospital of Zhengzhou University, Zhengzhou, Henan, People's Republic of China.
Department of Neurosurgery, The People's Hospital of Zhengzhou University, Zhengzhou, Henan, People's Republic of China
J Child Neurol. 2015 Jul;30(8):1017-23. doi: 10.1177/0883073814551795. Epub 2014 Oct 16.
Atypical teratoid/rhabdoid tumors are rare malignant pediatric brain tumors. This study was performed to characterize the clinicopathologic and neuroradiologic characteristics of atypical teratoid/rhabdoid tumors from 8 patients, including 5 male and 3 female infants (median age, 67 months). Neuroimaging revealed bulky masses of heterogeneous intensity with inhomogeneous enhancement. Three cases were infratentorial and 5 were supratentorial. Histopathologically, the tumors were predominantly composed of rhabdoid cells and undifferentiated small cells, mixed with some spindle or epithelial components. The tumors displayed striking polyphenotypic immunoreactivity, including varying degrees of positivity for vimentin, epithelial membrane antigen, smooth-muscle actin, cytokeratin, glial fibrillary acidic protein, neurofilament protein, synaptophysin, and CD99, and immunonegativity for desmin, placental alkaline phosphatase, and INI-1. The median survival duration was 9.5 months (range, 1-15 months) despite aggressive therapy. These results suggest that atypical teratoid/rhabdoid tumors display distinct clinicopathologic characteristics and indicate a poor prognosis. Immunohistochemistry facilitates the appropriate diagnosis of these tumors.
非典型畸胎样/横纹肌样肿瘤是罕见的儿童恶性脑肿瘤。本研究旨在描述8例非典型畸胎样/横纹肌样肿瘤患者的临床病理和神经放射学特征,其中包括5例男婴和3例女婴(中位年龄67个月)。神经影像学显示肿块体积较大,密度不均,强化不均匀。3例位于幕下,5例位于幕上。组织病理学上,肿瘤主要由横纹肌样细胞和未分化小细胞组成,混有一些梭形或上皮成分。肿瘤表现出显著的多表型免疫反应性,包括波形蛋白、上皮膜抗原、平滑肌肌动蛋白、细胞角蛋白、胶质纤维酸性蛋白、神经丝蛋白、突触素和CD99不同程度的阳性表达,以及结蛋白、胎盘碱性磷酸酶和INI-1的免疫阴性。尽管进行了积极治疗,中位生存期仍为9.5个月(范围1 - 15个月)。这些结果表明非典型畸胎样/横纹肌样肿瘤具有独特的临床病理特征,预后较差。免疫组织化学有助于对这些肿瘤进行准确诊断。