Stone John H, Brito-Zerón Pilar, Bosch Xavier, Ramos-Casals Manuel
Harvard Medical School, Boston, MA; Department of Medicine, Division of Rheumatology, Allergy, and Immunology, Massachusetts General Hospital, Boston, MA.
Josep Font Laboratory of Autoimmune Diseases, CELLEX-Institut d'Investigacions Biomèdiques August Pi i Sunyer (IDIBAPS), Barcelona, Spain; Department of Autoimmune Diseases, Hospital Clínic, University of Barcelona, Spain.
Mayo Clin Proc. 2015 Jul;90(7):927-39. doi: 10.1016/j.mayocp.2015.03.020.
IgG4-related disease (IgG4-RD) is a systemic disease characterized by the infiltration of IgG4-bearing plasma cells and, more importantly, distinctive histopathological features: storiform fibrosis, obliterative phlebitis, a lymphoplasmacytic infiltrate, and mild-to-moderate tissue eosinophilia. The diagnostic approach is complex and relies on the coexistence of various clinical, laboratory, and histopathological findings, none of which is pathognomonic in and of itself. IgG4-related disease should be suspected in patients presenting with unexplained enlargement or swelling of 1 or more organs or tissue organs. Four laboratory abnormalities often provide initial clues to the diagnosis of IgG4-RD: peripheral eosinophilia, hypergammaglobulinemia, elevated serum IgE levels, and hypocomplementemia. Elevated serum IgG4 levels provided critical information in identifying the first cases of IgG4-RD, but recent studies have reported substantial limitations to the measurement of serum IgG4 concentrations, precluding reliance on serum IgG4 concentrations for diagnostic purposes. In contrast, new studies have suggested a promising role of flow cytometry studies in the diagnosis and longitudinal management of IgG4-RD. Demonstration of the classic histopathological features of IgG4-RD remains crucial to diagnosis in most cases, and biopsy proof is preferred strongly by most disease experts before the initiation of treatment. Of note, the multiorgan nature of IgG4-RD was first established in 2003. This review intends to provide most recent knowledge about the clinical, laboratory, radiological, and pathological characteristics of IgG4-RD that may guide the physician to establish an early diagnosis. We searched PubMed and MEDLINE for relevant articles published between January 1, 2000, and November 1, 2014, using the search terms IgG4 and IgG4-related.
IgG4相关性疾病(IgG4-RD)是一种全身性疾病,其特征为携带IgG4的浆细胞浸润,更重要的是具有独特的组织病理学特征:席纹状纤维化、闭塞性静脉炎、淋巴浆细胞浸润以及轻度至中度组织嗜酸性粒细胞增多。诊断方法复杂,依赖于多种临床、实验室和组织病理学表现的共存,其中任何一项本身都不具有确诊意义。对于出现1个或多个器官或组织器官不明原因肿大或肿胀的患者,应怀疑IgG4相关性疾病。四项实验室异常常为IgG4-RD的诊断提供初步线索:外周血嗜酸性粒细胞增多、高球蛋白血症、血清IgE水平升高和补体减少。血清IgG4水平升高为识别首例IgG4-RD病例提供了关键信息,但最近的研究报告了血清IgG4浓度测量存在很大局限性,因此不能依赖血清IgG4浓度进行诊断。相比之下,新的研究表明流式细胞术研究在IgG4-RD的诊断和纵向管理中具有广阔前景。在大多数情况下,IgG4-RD经典组织病理学特征的显示对诊断仍然至关重要,并且大多数疾病专家在开始治疗前强烈倾向于活检证实。值得注意的是,IgG4-RD的多器官性质于2003年首次确立。本综述旨在提供有关IgG4-RD临床、实验室、放射学和病理学特征的最新知识,以指导医生早期诊断。我们使用搜索词IgG4和IgG4相关性,在PubMed和MEDLINE上搜索了2000年1月1日至2014年11月1日期间发表的相关文章。