Imbard Apolline, Benoist Jean-François, Esse Ruben, Gupta Sapna, Lebon Sophie, de Vriese An S, de Baulny Helene Ogier, Kruger Warren, Schiff Manuel, Blom Henk J
Biochemistry Hormonology Laboratory, Robert-Debré Hospital, APHP, 48 Bd Serurier, Paris 75019, France Paris Sud University, Pharmacy Faculty, 5 rue Jean Baptiste Clément, Chatenay-Malabry 92019, France
Biochemistry Hormonology Laboratory, Robert-Debré Hospital, APHP, 48 Bd Serurier, Paris 75019, France Paris Sud University, Pharmacy Faculty, 5 rue Jean Baptiste Clément, Chatenay-Malabry 92019, France.
Biosci Rep. 2015 Apr 28;35(4):e00222. doi: 10.1042/BSR20150094.
Betaine is the substrate of the liver- and kidney-specific betaine-homocysteine (Hcy) methyltransferase (BHMT), an alternate pathway for Hcy remethylation. We hypothesized that BHMT is a major pathway for homocysteine removal in cases of hyperhomocysteinaemia (HHcy). Therefore, we measured betaine in plasma and tissues from patients and animal models of HHcy of genetic and acquired cause. Plasma was collected from patients presenting HHcy without any Hcy interfering treatment. Plasma and tissues were collected from rat models of HHcy induced by diet and from a mouse model of cystathionine β-synthase (CBS) deficiency. S-adenosyl-methionine (AdoMet), S-adenosyl-homocysteine (AdoHcy), methionine, betaine and dimethylglycine (DMG) were quantified by ESI-LC-MS/MS. mRNA expression was quantified using quantitative real-time (QRT)-PCR. For all patients with diverse causes of HHcy, plasma betaine concentrations were below the normal values of our laboratory. In the diet-induced HHcy rat model, betaine was decreased in all tissues analysed (liver, brain, heart). In the mouse CBS deficiency model, betaine was decreased in plasma, liver, heart and brain, but was conserved in kidney. Surprisingly, BHMT expression and activity was decreased in liver. However, in kidney, BHMT and SLC6A12 expression was increased in CBS-deficient mice. Chronic HHcy, irrespective of its cause, induces betaine depletion in plasma and tissues (liver, brain and heart), indicating a global decrease in the body betaine pool. In kidney, betaine concentrations were not affected, possibly due to overexpression of the betaine transporter SLC6A12 where betaine may be conserved because of its crucial role as an osmolyte.
甜菜碱是肝脏和肾脏特异性甜菜碱-同型半胱氨酸(Hcy)甲基转移酶(BHMT)的底物,是Hcy再甲基化的一条替代途径。我们推测BHMT是高同型半胱氨酸血症(HHcy)患者体内同型半胱氨酸清除的主要途径。因此,我们检测了遗传和后天性病因导致的HHcy患者及动物模型血浆和组织中的甜菜碱。从未接受任何Hcy干扰治疗的HHcy患者中采集血浆。从饮食诱导的HHcy大鼠模型和胱硫醚β-合酶(CBS)缺乏的小鼠模型中采集血浆和组织。采用电喷雾电离液相色谱-串联质谱法(ESI-LC-MS/MS)对S-腺苷甲硫氨酸(AdoMet)、S-腺苷同型半胱氨酸(AdoHcy)、甲硫氨酸、甜菜碱和二甲基甘氨酸(DMG)进行定量分析。使用定量实时(QRT)-PCR对mRNA表达进行定量分析。对于所有病因各异的HHcy患者,血浆甜菜碱浓度均低于我们实验室的正常参考值。在饮食诱导的HHcy大鼠模型中,所分析的所有组织(肝脏、脑、心脏)中的甜菜碱均减少。在小鼠CBS缺乏模型中,血浆、肝脏、心脏和脑中的甜菜碱减少,但肾脏中的甜菜碱保持不变。令人惊讶的是,肝脏中BHMT的表达和活性降低。然而,在肾脏中,CBS缺乏小鼠的BHMT和SLC6A12表达增加。慢性HHcy,无论其病因如何,均会导致血浆和组织(肝脏、脑和心脏)中的甜菜碱耗竭,表明体内甜菜碱池整体减少。在肾脏中,甜菜碱浓度未受影响,这可能是由于甜菜碱转运体SLC6A12的过表达,因其作为渗透溶质的关键作用,甜菜碱在肾脏中得以保留。