Higashi Kenjiro, Ogawa Takenori, Onuma Masaei, Usubuchi Hajime, Imai Yoshimichi, Takata Iori, Hidaka Hiroshi, Watanabe Mika, Sasahara Yoji, Koyama Shigeto, Kure Shigeo, Katori Yukio
Department of Otolaryngology-Head and Neck Surgery, Tohoku University Graduate School of Medicine, 2-1 Seiryo-machi, Aoba-ku, Sendai, Miyagi 980-8575, Japan.
Department of Otolaryngology-Head and Neck Surgery, Tohoku University Graduate School of Medicine, 2-1 Seiryo-machi, Aoba-ku, Sendai, Miyagi 980-8575, Japan.
Auris Nasus Larynx. 2016 Aug;43(4):451-4. doi: 10.1016/j.anl.2015.10.010. Epub 2015 Nov 18.
Melanotic neuroectodermal tumor of infancy (MNTI) is an extremely rare, pigmented neoplastic entity of neural crest origin. Histological and immunohistochemical profiles indicate the presence of two components, small rounded neuroblast-like cellular areas and areas with large melanin-containing cells which consist of combination of neural, melanocytic, and epithelial cell types. Here we present two interesting cases of infants with MNTI which have different clinicopathological features. The first case is a 3-month-old female with rapidly growing MNTI involving the lacrimal sac and inferior wall of the orbital cavity, treated with total maxillectomy without orbital exenteration followed by chemotherapy. The second case is a 7-month-old male with slow-growing maxillary MNTI treated with complete surgical excision. In the female patient, histological findings revealed a predominance of neuroblast-like cellular areas and a high Ki67 index indicating rapid cellular proliferation. In the male patient however, large melanin-containing cells were dominant in this slow-growing tumor. These findings support the presence of two different types of MNTI, rapid-growing and slow-growing types, determined by the component of neuroblast-like cellular areas.
婴儿黑色素性神经外胚层肿瘤(MNTI)是一种极为罕见的、起源于神经嵴的色素性肿瘤实体。组织学和免疫组化特征显示存在两种成分,即小的圆形神经母细胞样细胞区域和含有大量黑色素细胞的区域,后者由神经、黑素细胞和上皮细胞类型组合而成。在此,我们呈现两例具有不同临床病理特征的婴儿MNTI有趣病例。第一例是一名3个月大的女性,患有快速生长的MNTI,累及泪囊和眶腔下壁,接受了全上颌骨切除术,未行眶内容剜除术,随后进行了化疗。第二例是一名7个月大的男性,患有生长缓慢的上颌MNTI,接受了完整的手术切除。在女性患者中,组织学检查结果显示神经母细胞样细胞区域占优势,且Ki67指数较高,表明细胞增殖迅速。然而,在男性患者中,在这种生长缓慢的肿瘤中,含大量黑色素的细胞占主导。这些发现支持存在两种不同类型的MNTI,即快速生长型和缓慢生长型,这由神经母细胞样细胞区域的成分决定。