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一例罕见的由低拷贝重复序列3/4侧翼的10q22.3q23.2微缺失新病例。

A New Case of the Rare 10q22.3q23.2 Microdeletion Flanked by Low-Copy Repeats 3/4.

作者信息

Coelho Molck Miriam, Simioni Milena, Paiva Vieira Társis, Paoli Monteiro Fabíola, Gil-da-Silva-Lopes Vera L

机构信息

Department of Medical Genetics, Faculty of Medical Sciences, University of Campinas (UNICAMP), Campinas, Brazil.

出版信息

Mol Syndromol. 2017 May;8(3):161-167. doi: 10.1159/000469965. Epub 2017 Apr 19.

Abstract

Deletions in the 10q22.3q23.2 region are rare and mediated by 2 low-copy repeats (LCRs 3 and 4). These deletions have already been recognized as the 10q22q23 deletion syndrome. The phenotype associated with this condition is rather uncharacteristic, and most common features are craniofacial dysmorphisms and developmental delay. We describe a boy with craniofacial dysmorphic features, developmental delay, tetralogy of Fallot, hand/foot abnormalities, and recurrent respiratory tract infections. Chromosomal microarray analysis disclosed a 7.8-Mb microdeletion at 10q22.3q23.2, flanked by LCRs 3/4, and an additional 16q12.1 microdeletion of 189 kb. This article reviews the clinical signs of reported cases with similar deletions and compares them with our patient, contributing to a better understanding of genotype-phenotype correlation.

摘要

10q22.3q23.2区域的缺失较为罕见,由两个低拷贝重复序列(LCR 3和LCR 4)介导。这些缺失已被确认为10q22q23缺失综合征。与该病症相关的表型相当不典型,最常见的特征是颅面部畸形和发育迟缓。我们描述了一名患有颅面部畸形特征、发育迟缓、法洛四联症、手足异常和反复呼吸道感染的男孩。染色体微阵列分析显示在10q22.3q23.2区域有一个7.8兆碱基的微缺失,两侧为LCR 3/4,另外在16q12.1区域有一个189千碱基的微缺失。本文回顾了报道的具有类似缺失病例的临床体征,并将其与我们的患者进行比较,有助于更好地理解基因型 - 表型相关性。

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