Harumatsu Toshio, Uchida Goki, Fujimura Takumi, Kato Mototoshi, Tomita Hirofumi, Ishioka Shigeki, Shimotakahara Akihiro, Shimojima Naoki, Ieiri Satoshi, Hirobe Seiichi
Department of Surgery, Tokyo Metropolitan Children's Medical Center, 2-8-29 Musashidai, fuchyu, Tokyo 183-0042, Japan; Department of Pediatric Surgery, Research Field in Medicine and Health Sciences, Medical and Dental Sciences Area, Research and Education Assembly, Kagoshima University, 8-35-1, Sakuragaoka, Kagoshima City, 890-8520, Japan.
Department of Surgery, Tokyo Metropolitan Children's Medical Center, 2-8-29 Musashidai, fuchyu, Tokyo 183-0042, Japan.
J Pediatr Surg. 2019 Apr;54(4):766-770. doi: 10.1016/j.jpedsurg.2018.12.009. Epub 2019 Jan 23.
Lingual thyroglossal duct cysts (L-TGDCs) are rare and sometimes lethal owing to their association with asphyxia. We aimed to analyze our single institutional experience with L-TGDCs.
Twelve L-TGDC cases treated at our institution between January 2010 and December 2017 were investigated.
The male/female ratio was 6/6. The age at the diagnosis was 2 ± 1.4 months (7 days to 6 months), and 3 patients were diagnosed in the neonatal period. The patients presented with stridor (n = 12; 100%), growth retardation (n = 5; 42%), apnea (n = 3; 25%), and vomiting (n = 1; 8.3%). Lateral X-rays were obtained in 8 cases (66.7%); a lingual mass was suspected in 7 (87.5%). Transoral marsupialization of the cyst was performed under direct vision in all cases. All cases were nasally and orally intubated using a laryngoscope, bronchoscope, or airway scope. The mean operative time was 18 ± 2.9 min. The mean cyst size was 10.5 ± 1.8 mm. No recurrence was observed during the follow-up period (37.5 ± 18 months).
L-TGDC requires a precise diagnosis and rapid intervention because of the risk of asphyxia resulting in sudden death. Transoral marsupialization under direct vision is an effective and secure approach. L-TGDC should be considered when patients younger than six months of age present with respiratory distress.
Retrospective Study.
Level IV.
舌甲状腺舌管囊肿(L-TGDCs)较为罕见,有时因与窒息相关而具有致命性。我们旨在分析我们单机构治疗L-TGDCs的经验。
对2010年1月至2017年12月在我们机构治疗的12例L-TGDC病例进行调查。
男女比例为6/6。诊断时的年龄为2±1.4个月(7天至6个月),3例患者在新生儿期被诊断。患者表现为喘鸣(n = 12;100%)、生长发育迟缓(n = 5;42%)、呼吸暂停(n = 3;25%)和呕吐(n = 1;8.3%)。8例(66.7%)进行了侧位X线检查;7例(87.5%)怀疑有舌部肿物。所有病例均在直视下进行囊肿经口袋形缝合术。所有病例均使用喉镜、支气管镜或气道镜进行鼻腔和口腔插管。平均手术时间为18±2.9分钟。囊肿平均大小为10.5±1.8毫米。随访期间(37.5±18个月)未观察到复发。
由于存在窒息导致猝死的风险,L-TGDC需要精确诊断和快速干预。直视下经口袋形缝合术是一种有效且安全的方法。6个月以下出现呼吸窘迫的患者应考虑L-TGDC。
回顾性研究。
四级。