Unusual urethral duplication.

Urethral duplication is a rare congenital anomaly occurring almost exclusively in males. The described varieties include the sagital (Y-duplication), spindle, epispadiac, hypospadiac, complete, incomplete, abortive and collateral duplications. Whereas over 150 cases of this anomaly have been reported in the world literature, the associated findings of an adenocarcinoma of the urinary bladder and a urethral calculus have not been previously encountered. This case report describes the clinical presentation, the extraordinary intraoperative finding of an adenocarcinoma of the fundus of the urinary bladder, the investigative procedures, the management and follow-up of this most unusual complete urethral duplication.